Document Detail


A new neurocutaneous syndrome possibly related to Ota's nevus.
MedLine Citation:
PMID:  8229056     Owner:  NLM     Status:  MEDLINE    
Abstract/OtherAbstract:
The case of a 42-year-old Sudanese man is reported who had developed hyperpigmentation of the left face and rapidly progressive right hemiparesis followed by myoclonus at the age of 30. Blue-grey hyperpigmentation was noted in the territory of the left ophthalmic, maxillary and mandibular trigeminal nerve branches, with alopecia of the right face and axilla. CT of the brain revealed left-sided paraventricular calcifications and MRI showed atrophy of the left cerebral hemisphere and mesencephalon, a calcified haemangioma in the left basal ganglia, an old infarct in the right central pons, and cerebellar atrophy. This case resembles Ota's syndrome; however, atypical distribution of the facial nevus, the epidermal location of hyperpigmentation, and the combination of vascular and degenerative cerebral malformations indicate that this is a new hitherto unreported neurocutaneous vascular syndrome.
Authors:
S M al Deeb; Y Bahou
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Publication Detail:
Type:  Case Reports; Journal Article    
Journal Detail:
Title:  Journal of the neurological sciences     Volume:  118     ISSN:  0022-510X     ISO Abbreviation:  J. Neurol. Sci.     Publication Date:  1993 Aug 
Date Detail:
Created Date:  1993-12-03     Completed Date:  1993-12-03     Revised Date:  2004-11-17    
Medline Journal Info:
Nlm Unique ID:  0375403     Medline TA:  J Neurol Sci     Country:  NETHERLANDS    
Other Details:
Languages:  eng     Pagination:  92-6     Citation Subset:  IM    
Affiliation:
Department of Clinical Neurosciences, Riyadh Armed Forces Hospital, Saudi Arabia.
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MeSH Terms
Descriptor/Qualifier:
Adult
Atrophy
Brain / pathology,  radionuclide imaging
Electroencephalography
Humans
Hyperpigmentation / pathology*
Magnetic Resonance Imaging
Male
Nervous System Diseases / pathology*,  physiopathology,  radiography
Nevus of Ota / pathology*,  physiopathology,  radiography
Syndrome
Tomography, X-Ray Computed

From MEDLINE®/PubMed®, a database of the U.S. National Library of Medicine


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