Document Detail


The first Chinese Pierson syndrome with novel mutations in LAMB2.
MedLine Citation:
PMID:  19861315     Owner:  NLM     Status:  MEDLINE    
Abstract/OtherAbstract:
BACKGROUND: Pierson syndrome is typically manifested with congenital nephrotic syndrome (CNS) and peculiar ocular changes. LAMB2 was the causative gene. METHODS: A 3.25-year-old girl presenting with childhood-onset heavy proteinuria, bilateral myosis and nystagmus was detected on mutations of LAMB2 gene by PCR direct sequencing. RESULTS: Two novel mutations were identified, C757fsX767 and P1413fsX1451, which predicted truncated proteins and were confirmed in the paternal and maternal origins, respectively. CONCLUSIONS: This is the first Chinese case of Pierson syndrome diagnosed by clinical manifestations and LAMB2 gene mutations. The phenotype may be different in different ethics.
Authors:
Dan Zhao; Jie Ding; Fang Wang; Qingfeng Fan; Na Guan; Suxia Wang; Yan Zhang
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Publication Detail:
Type:  Case Reports; Journal Article; Research Support, Non-U.S. Gov't     Date:  2009-10-26
Journal Detail:
Title:  Nephrology, dialysis, transplantation : official publication of the European Dialysis and Transplant Association - European Renal Association     Volume:  25     ISSN:  1460-2385     ISO Abbreviation:  Nephrol. Dial. Transplant.     Publication Date:  2010 Mar 
Date Detail:
Created Date:  2010-02-26     Completed Date:  2010-06-03     Revised Date:  -    
Medline Journal Info:
Nlm Unique ID:  8706402     Medline TA:  Nephrol Dial Transplant     Country:  England    
Other Details:
Languages:  eng     Pagination:  776-8     Citation Subset:  IM    
Affiliation:
Department of Pediatrics, Peking University First Hospital, Beijing 100034, PR China.
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MeSH Terms
Descriptor/Qualifier:
Child, Preschool
China
Eye Abnormalities / ethnology,  genetics*
Female
Gene Deletion
Humans
Kidney Diseases / congenital*,  ethnology,  genetics*
Laminin / genetics*
Mutation / genetics*
Nystagmus, Congenital / ethnology,  genetics*
Proteinuria / genetics
Syndrome
Chemical
Reg. No./Substance:
0/Laminin; 124148-86-3/laminin beta2

From MEDLINE®/PubMed®, a database of the U.S. National Library of Medicine


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