Document Detail


A child with hemimegalencephaly, hemihypertrophy, macrocephaly, cutaneous vascular malformation, psychomotor retardation and intestinal lymphangiectasia--a diagnostic dilemma.
MedLine Citation:
PMID:  10532178     Owner:  NLM     Status:  MEDLINE    
Abstract/OtherAbstract:
Although the clinical delineation of the majority of overgrowth syndromes is straightforward, we believe there is a subset of patients with overlapping features from a number of overgrowth syndromes. We report a patient with hemimegalencephaly, hemihypertrophy, macrocephaly, vascular lesions, psychomotor retardation and intestinal lymphangiectasia. The clinical history and findings posed a diagnostic dilemma as the features overlapped between several conditions, namely macrocephaly-cutis marmorata telangiectatica congenita (M-CMTC), Klippel-Trenaunay-Weber syndrome (KTWS), Proteus syndrome and a provisional unique syndrome described by Reardon et al. (1996, Am J Med Genet 66:144-149). We anticipate that only when the molecular basis is delineated will it become clear whether these disorders are separate entities or merely differing ends of the same spectrum.
Authors:
M K Thong; E Thompson; R Keenan; K Simmer; M Harbord; G Davidson; E Haan
Related Documents :
15984958 - Klippel-trenaunay syndrome.
3780268 - Intracranial gyriform calcification associated with subarachnoid fat.
9613758 - Erdheim-chester disease with extensive intraaxial brain stem lesions presenting as a pr...
1669958 - Successful treatment of kasabach-merritt syndrome with prednisone and epsilon-aminocapr...
17494788 - Obstructive sleep apnea syndrome is associated with some components of metabolic syndrome.
8193408 - A case of hutchinson-gilford progeria syndrome mimicking scleredema in early infancy.
Publication Detail:
Type:  Journal Article    
Journal Detail:
Title:  Clinical dysmorphology     Volume:  8     ISSN:  0962-8827     ISO Abbreviation:  Clin. Dysmorphol.     Publication Date:  1999 Oct 
Date Detail:
Created Date:  1999-11-16     Completed Date:  1999-11-16     Revised Date:  2004-11-17    
Medline Journal Info:
Nlm Unique ID:  9207893     Medline TA:  Clin Dysmorphol     Country:  ENGLAND    
Other Details:
Languages:  eng     Pagination:  283-6     Citation Subset:  IM    
Affiliation:
South Australian Clinical Genetics Service, Women's and Children's Hospital, North Adelaide, Australia. thongmk@mail.wch.sa.gov.au
Export Citation:
APA/MLA Format     Download EndNote     Download BibTex
MeSH Terms
Descriptor/Qualifier:
Abnormalities, Multiple*
Child, Preschool
Developmental Disabilities*
Head / abnormalities*
Humans
Intestines / abnormalities*
Lymphangiectasis / congenital*
Male
Pigmentation Disorders
Psychomotor Performance
Skin / blood supply*

From MEDLINE®/PubMed®, a database of the U.S. National Library of Medicine


Previous Document:  Disorganisation: a case with popliteal pterygia and placental-skin appendages.
Next Document:  Bilateral hydronephrosis due to megacalicosis as a prenatal sonographic finding in a female with Sch...