Document Detail


A case of congenital nephrotic syndrome associated with partial deficiency of lecithin cholesterol acyltransferase (LCAT) and hypothyroidism.
MedLine Citation:
PMID:  6500816     Owner:  NLM     Status:  MEDLINE    
Abstract/OtherAbstract:
The case of a 3 year-old boy with congenital nephrotic syndrome is reported, in whom decreased LCAT activity and hypothyroidism were also present. Renal biopsy confirmed a diffuse proliferative glomerulonephritis with a large number of foam cells in the capillary lumen of the glomerulus and the interstitium, which stained positively with acid phosphatase indicating the presence of macrophage with phagocyted lipid vacuole. The histological picture was similar to that of familial LCAT deficiency, but the reported case is one of secondary LCAT deficiency as a result of urinary loss of the enzyme. Replacement therapy with thyroid hormones resulted in improvement in growth and development.
Authors:
M Hiramatsu; S Karashima; S Hattori; I Matsuda; H Maeda
Related Documents :
7204936 - Genetic variation in the terrestrial isopod, armadillidium vulgare.
617966 - Hypertriglyceridemia in homozygous beta-thalassemia.
694426 - Reversible severe anaemia and granulocytopenia caused by procainamide. a case report.
7428176 - An unusual case of mannosidosis with severe deficiency of acid mannosidase in leukocyte...
15660236 - A case of idiopathic hypertrophic cranial pachymeningitis manifested only by positive r...
19261556 - The changing nature of rectus sheath haematoma: case series and literature review.
Publication Detail:
Type:  Case Reports; Journal Article    
Journal Detail:
Title:  The International journal of pediatric nephrology     Volume:  5     ISSN:  0391-6510     ISO Abbreviation:  Int J Pediatr Nephrol     Publication Date:  1984 Sep 
Date Detail:
Created Date:  1985-01-09     Completed Date:  1985-01-09     Revised Date:  2006-11-15    
Medline Journal Info:
Nlm Unique ID:  8007162     Medline TA:  Int J Pediatr Nephrol     Country:  ITALY    
Other Details:
Languages:  eng     Pagination:  183-6     Citation Subset:  IM    
Export Citation:
APA/MLA Format     Download EndNote     Download BibTex
MeSH Terms
Descriptor/Qualifier:
Child, Preschool
Humans
Hyperlipidemias / etiology
Hypolipoproteinemias / etiology*
Hypothyroidism / etiology*
Lecithin Acyltransferase Deficiency / etiology*
Lipoproteins / blood
Male
Nephrotic Syndrome / complications,  congenital*
Proteinuria / etiology
Serum Albumin / metabolism
Chemical
Reg. No./Substance:
0/Lipoproteins; 0/Serum Albumin

From MEDLINE®/PubMed®, a database of the U.S. National Library of Medicine


Previous Document:  Renal infarction--a rare complication of Schönlein-Henoch syndrome.
Next Document:  Therapy after stroke: amounts, determinants and effects.