Document Detail


Tumoral calcinosis due to GALNT3 C.516-2A >T mutation in a black African family.
MedLine Citation:
PMID:  18618993     Owner:  NLM     Status:  MEDLINE    
Abstract/OtherAbstract:
Familial Tumoral Calcinosis (FTC) is a rare autosomal recessive disorder of the phosphocalcic metabolism caused by mutations in the FGF23 or GALNT3 genes. We have identified a Beninese family in which two brothers present FTC caused by a homozygous A>T transversion at the acceptor splice site in intron 1 of GALNT3 gene. We report on the clinical, biochemical, histopathological and molecular spectrum of the disorder in this family. The particularly severe phenotype, the amelogenesis imperfecta, and the carbapatite deposit observed in these patients, seem to be characteristic of our observations.
Authors:
A Laleye; M J Alao; G Gbessi; M Adjagba; M Marche; I Coupry; I Redonnet-Vernhet; S Lepreux; B Ayivi; R B Darboux; D Lacombe; B Arveiler
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Publication Detail:
Type:  Case Reports; Journal Article; Research Support, Non-U.S. Gov't    
Journal Detail:
Title:  Genetic counseling (Geneva, Switzerland)     Volume:  19     ISSN:  1015-8146     ISO Abbreviation:  Genet. Couns.     Publication Date:  2008  
Date Detail:
Created Date:  2008-07-14     Completed Date:  2008-09-09     Revised Date:  2008-10-28    
Medline Journal Info:
Nlm Unique ID:  9015261     Medline TA:  Genet Couns     Country:  Switzerland    
Other Details:
Languages:  eng     Pagination:  183-92     Citation Subset:  IM    
Affiliation:
Unité de Biologie Humaine, Faculté des Sciences de la Santé, Cotonou, Bénin. cytogen@intnet.bj
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MeSH Terms
Descriptor/Qualifier:
Adolescent
Adult
African Continental Ancestry Group / genetics*
Amelogenesis Imperfecta / genetics,  pathology
Apatites / blood
Benin
Calcinosis / genetics*,  pathology
Humans
Hyperphosphatemia / genetics,  pathology
Joint Diseases / genetics*,  pathology
Male
Mutation*
N-Acetylgalactosaminyltransferases / genetics*
Pedigree
Siblings
Chemical
Reg. No./Substance:
0/Apatites; EC 2.4.1.-/N-Acetylgalactosaminyltransferases; EC 2.4.1.41/polypeptide N-acetylgalactosaminyltransferase

From MEDLINE®/PubMed®, a database of the U.S. National Library of Medicine


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