Document Detail


T-cell acute lymphoblastic leukemia in association with Börjeson-Forssman-Lehmann syndrome due to a mutation in PHF6.
MedLine Citation:
PMID:  20806366     Owner:  NLM     Status:  MEDLINE    
Abstract/OtherAbstract:
Börjeson-Forssman-Lehmann syndrome (BFLS) is a rare X-linked mental retardation syndrome that is caused by germline mutations in PHF6. We describe a 9-year-old male with BFLS, who developed T-cell acute lymphoblastic leukemia (T-ALL). The PHF6 gene is located on the X chromosome and encodes a protein with two PHD-type zinc finger domains and four nuclear localization sequences. Previously, overexpression of Phf6 was observed in murine T-cell lymphomas. Our observation indicates that BFLS may represent a cancer predisposition syndrome and that mutations of PHF6 contribute to T-ALL.
Authors:
Mwe Mwe Chao; Matthew A Todd; Udo Kontny; Katherine Neas; Michael J Sullivan; Alasdair G Hunter; David J Picketts; Christian P Kratz
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Publication Detail:
Type:  Case Reports; Journal Article; Research Support, N.I.H., Intramural; Research Support, Non-U.S. Gov't    
Journal Detail:
Title:  Pediatric blood & cancer     Volume:  55     ISSN:  1545-5017     ISO Abbreviation:  Pediatr Blood Cancer     Publication Date:  2010 Oct 
Date Detail:
Created Date:  2010-08-31     Completed Date:  2010-09-27     Revised Date:  2011-10-03    
Medline Journal Info:
Nlm Unique ID:  101186624     Medline TA:  Pediatr Blood Cancer     Country:  United States    
Other Details:
Languages:  eng     Pagination:  722-4     Citation Subset:  IM    
Copyright Information:
Copyright 2010 Wiley-Liss, Inc.
Affiliation:
Division of Pediatric Hematology-Oncology, Children's National Medical Center, Washington, District of Columbia, USA.
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MeSH Terms
Descriptor/Qualifier:
Carrier Proteins / genetics*
Child
Humans
Male
Mental Retardation, X-Linked / genetics*
Mutation*
Precursor T-Cell Lymphoblastic Leukemia-Lymphoma / genetics*
Grant Support
ID/Acronym/Agency:
//Canadian Institutes of Health Research
Chemical
Reg. No./Substance:
0/Carrier Proteins; 0/PHF6 protein, human
Comments/Corrections
Comment In:
Pediatr Blood Cancer. 2010 Oct;55(4):595-6   [PMID:  20589626 ]

From MEDLINE®/PubMed®, a database of the U.S. National Library of Medicine


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