Document Detail


Successful treatment of Kasabach-Merritt syndrome with prednisone and epsilon-aminocaproic acid.
MedLine Citation:
PMID:  1669958     Owner:  NLM     Status:  MEDLINE    
Abstract/OtherAbstract:
The Kasabach-Merritt syndrome is characterized by thrombocytopenia and localized coagulopathy associated with a hemangioma. Most techniques applied to eradicate the tumor or accelerate its involution (surgery, radiation therapy, embolization) are invasive and require transfusion of large amounts of blood products. In some cases, medical treatment is the only alternative. Efficacy of steroids and antifibronolytic agents has already been described, but even this approach is associated with the administration of blood products. We report two cases of infants with Kasabach-Merritt syndrome associated with cardiac and hepatic hemangiomas. At admission, both had signs of cardiac failure. They were successfully treated with prednisone and epsilon-aminocaproic acid (EACA). Blood products were not required once the diagnosis was made. These observations have important implications for the management of patients with Kasabach-Merritt syndrome because they show that even in severe cases blood transfusions can be avoided by the use of prednisone and EACA.
Authors:
M F Dresse; M David; H Hume; H Blanchard; P Russo; N Van Doesberg; G E Rivard
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Publication Detail:
Type:  Case Reports; Journal Article; Research Support, Non-U.S. Gov't    
Journal Detail:
Title:  Pediatric hematology and oncology     Volume:  8     ISSN:  0888-0018     ISO Abbreviation:  Pediatr Hematol Oncol     Publication Date:    1991 Oct-Dec
Date Detail:
Created Date:  1992-03-18     Completed Date:  1992-03-18     Revised Date:  2007-11-15    
Medline Journal Info:
Nlm Unique ID:  8700164     Medline TA:  Pediatr Hematol Oncol     Country:  ENGLAND    
Other Details:
Languages:  eng     Pagination:  329-34     Citation Subset:  IM    
Affiliation:
Hematology-Oncology, Hôpital Sainte-Justine, Montreal, Quebec, Canada.
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MeSH Terms
Descriptor/Qualifier:
6-Aminocaproic Acid / therapeutic use*
Disseminated Intravascular Coagulation / drug therapy*
Drug Therapy, Combination
Female
Heart Failure / drug therapy
Heart Neoplasms / drug therapy
Hemangioma / drug therapy*
Humans
Infant
Infant, Newborn
Liver Neoplasms / drug therapy
Male
Prednisone / therapeutic use*
Syndrome
Thrombocytopenia / drug therapy*
Chemical
Reg. No./Substance:
53-03-2/Prednisone; 60-32-2/6-Aminocaproic Acid
Comments/Corrections
Comment In:
Pediatr Hematol Oncol. 1993 Apr-Jun;10(2):197-8   [PMID:  8318377 ]

From MEDLINE®/PubMed®, a database of the U.S. National Library of Medicine


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