Document Detail


Spondyloepimetaphyseal dysplasia (SEMD) Shohat type.
MedLine Citation:
PMID:  8074146     Owner:  NLM     Status:  MEDLINE    
Abstract/OtherAbstract:
Recently a distinct spondyloepimetaphyseal dysplasia (SEMD) was reported in three members of a Jewish family. We present a 3.5-year-old Mexican boy with disproportionate short stature, peculiar face, short neck, small chest, abdominal distension, lumbar lordosis, short limbs, marked genua vara, and joint laxity. Roentgenologic findings include short long bones, wide and flared metaphyses with irregularities, delayed epiphyseal ossification, platyspondyly and morphological changes of vertebral bodies and fibular overgrowth. The striking resemblance of this patient to those previously reported confirms this form of SEMD as a distinct entity. Autosomal recessive inheritance is supported and the designation SEMD Shohat type is proposed.
Authors:
L E Figuera; M L Ramírez-Dueñas; M P Gallegos-Arreola; J M Cantú
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Publication Detail:
Type:  Case Reports; Journal Article    
Journal Detail:
Title:  American journal of medical genetics     Volume:  51     ISSN:  0148-7299     ISO Abbreviation:  Am. J. Med. Genet.     Publication Date:  1994 Jul 
Date Detail:
Created Date:  1994-09-23     Completed Date:  1994-09-23     Revised Date:  2004-11-17    
Medline Journal Info:
Nlm Unique ID:  7708900     Medline TA:  Am J Med Genet     Country:  UNITED STATES    
Other Details:
Languages:  eng     Pagination:  213-5     Citation Subset:  IM    
Affiliation:
División de Genética, Centro de Investigación Biomédica de Occidente, IMSS, Guadalajara, México.
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MeSH Terms
Descriptor/Qualifier:
Abnormalities, Multiple / genetics*
Child, Preschool
Dwarfism / congenital
Fibula / abnormalities*
Genes, Recessive
Humans
Hypertrophy
Joint Instability
Knee Joint / physiopathology
Lordosis / genetics
Male
Osteochondrodysplasias / genetics*,  pathology

From MEDLINE®/PubMed®, a database of the U.S. National Library of Medicine


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