Document Detail


Psychological well-being in parents of children with Angelman, Cornelia de Lange and Cri du Chat syndromes.
MedLine Citation:
PMID:  21323782     Owner:  NLM     Status:  Publisher    
Abstract/OtherAbstract:
Background  The current study focuses on mothers and fathers of children with three rare genetic syndromes that are relatively unexplored in terms of family experience: Angelman syndrome, Cornelia de Lange syndrome and Cri du Chat syndrome. Method  Parents of children with Angelman syndrome (n = 15), Cornelia de Lange syndrome (n = 16) and Cri du Chat syndrome (n = 18), and a matched comparison group of parents of children with autism and intellectual disabilities (n = 20) completed questionnaires on both psychological distress (stress, anxiety, depression) and positive psychological functioning. Results  Parents of children with Angelman syndrome consistently reported the highest levels of psychological distress, and parents of children with Cornelia de Lange syndrome the lowest, with parents of children with Cri du Chat syndrome and autism scoring between these two. Positive psychological functioning was similar across the four aetiology groups. Conclusions  Parents of children with rare genetic syndromes are at risk for high levels of stress and mental health problems. Methodological issues and the practical applications of these results are discussed.
Authors:
G M Griffith; R P Hastings; C Oliver; P Howlin; J Moss; J Petty; P Tunnicliffe
Publication Detail:
Type:  JOURNAL ARTICLE     Date:  2011-2-15
Journal Detail:
Title:  Journal of intellectual disability research : JIDR     Volume:  -     ISSN:  1365-2788     ISO Abbreviation:  -     Publication Date:  2011 Feb 
Date Detail:
Created Date:  2011-2-17     Completed Date:  -     Revised Date:  -    
Medline Journal Info:
Nlm Unique ID:  9206090     Medline TA:  J Intellect Disabil Res     Country:  -    
Other Details:
Languages:  ENG     Pagination:  -     Citation Subset:  -    
Copyright Information:
© 2011 The Authors. Journal of Intellectual Disability Research © 2011 Blackwell Publishing Ltd.
Affiliation:
School of Psychology, Bangor University, Bangor, UK School of Psychology, University of Birmingham, Birmingham, UK Department of Psychology, Institute of Psychiatry, London, UK.
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