Document Detail


Proton MR spectroscopy in succinic semialdehyde dehydrogenase deficiency.
MedLine Citation:
PMID:  15037717     Owner:  NLM     Status:  MEDLINE    
Abstract/OtherAbstract:
Succinic semialdehyde dehydrogenase (SSADH) deficiency is a rare hereditary disorder of the CNS catabolism of gamma-aminobutyric acid (GABA), leading to accumulation of the metabolite 4-hydroxybutyrate (GHB). Here the authors report on 1.5 and 3.0 T proton MR spectroscopy in a patient with SSADH deficiency. A characteristic pattern with clearly elevated GABA levels and traces of GHB was found in both the white and the gray matter of the brain. In vivo spectroscopy may be useful for diagnosis and monitoring SSADH deficiency.
Authors:
T Ethofer; U Seeger; U Klose; M Erb; B Kardatzki; E Kraft; G B Landwehrmeyer; W Grodd; A Storch
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Publication Detail:
Type:  Case Reports; Journal Article; Research Support, Non-U.S. Gov't    
Journal Detail:
Title:  Neurology     Volume:  62     ISSN:  1526-632X     ISO Abbreviation:  Neurology     Publication Date:  2004 Mar 
Date Detail:
Created Date:  2004-03-23     Completed Date:  2004-07-19     Revised Date:  2006-11-15    
Medline Journal Info:
Nlm Unique ID:  0401060     Medline TA:  Neurology     Country:  United States    
Other Details:
Languages:  eng     Pagination:  1016-8     Citation Subset:  AIM; IM    
Affiliation:
Section on Experimental MR of the CNS, Department of Neuroradiology, University of Tübingen, Germany.
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MeSH Terms
Descriptor/Qualifier:
Adult
Aldehyde Oxidoreductases / deficiency*,  genetics,  metabolism
Amino Acid Metabolism, Inborn Errors / diagnosis*,  enzymology*,  genetics
Brain / enzymology,  metabolism
Genes, Recessive
Glutamic Acid / metabolism
Glutamine / metabolism
Humans
Hydroxybutyrates / metabolism
Magnetic Resonance Spectroscopy / methods*
Male
Movement Disorders / enzymology,  genetics
Predictive Value of Tests
Protons
Reference Values
Seizures / enzymology,  genetics
Speech Disorders / enzymology,  genetics
Succinate-Semialdehyde Dehydrogenase
gamma-Aminobutyric Acid / metabolism*
Chemical
Reg. No./Substance:
0/Hydroxybutyrates; 0/Protons; 56-12-2/gamma-Aminobutyric Acid; 56-85-9/Glutamine; 56-86-0/Glutamic Acid; 591-81-1/4-hydroxybutyric acid; EC 1.2.-/Aldehyde Oxidoreductases; EC 1.2.1.24/ALDH5A1 protein, human; EC 1.2.1.24/Succinate-Semialdehyde Dehydrogenase

From MEDLINE®/PubMed®, a database of the U.S. National Library of Medicine


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