Document Detail


Prevalence and clinical characteristics of lymphangioleiomyomatosis (LAM) in patients with tuberous sclerosis complex.
MedLine Citation:
PMID:  11520735     Owner:  NLM     Status:  MEDLINE    
Abstract/OtherAbstract:
The true prevalence of pulmonary lymphangioleiomyomatosis (LAM) in patients with tuberous sclerosis complex (TSC) is unknown. The prevalence of LAM, radiological features, and lung function in patients with TSC was measured. The presence of LAM, as defined by the presence of cysts by high-resolution chest computed tomography (HRCT) scan, was determined in patients with TSC without prior pulmonary disease (Group 1). To determine the significance of early detection, severity of disease in screened patients (Group 1) was compared with that in patients with TSC with a prior diagnosis of LAM (Group 2). Forty-eight patients with TSC and no prior history of LAM were screened. Of the 38 females, 13 (34%) had LAM; LAM was absent in males. Lung function was preserved in patients with TSC who were found to have LAM by screening. In patients previously known to have LAM, FEV(1) and DL(CO) correlated inversely with severity of disease as assessed by CT scan. The prevalence of LAM in women with TSC was 34%, approximately 10-fold that previously reported, consistent with a large hitherto unrecognized subclinical population of patients at risk for pulmonary complications.
Authors:
J Moss; N A Avila; P M Barnes; R A Litzenberger; J Bechtle; P G Brooks; C J Hedin; S Hunsberger; A S Kristof
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Publication Detail:
Type:  Journal Article; Research Support, U.S. Gov't, P.H.S.    
Journal Detail:
Title:  American journal of respiratory and critical care medicine     Volume:  164     ISSN:  1073-449X     ISO Abbreviation:  Am. J. Respir. Crit. Care Med.     Publication Date:  2001 Aug 
Date Detail:
Created Date:  2001-08-24     Completed Date:  2001-10-11     Revised Date:  2006-11-15    
Medline Journal Info:
Nlm Unique ID:  9421642     Medline TA:  Am J Respir Crit Care Med     Country:  United States    
Other Details:
Languages:  eng     Pagination:  669-71     Citation Subset:  AIM; IM    
Affiliation:
Pulmonary-Critical Care Medicine Branch, National Heart, Lung, and Blood Institute, Diagnostic Radiology Department, Warren G. Magnuson Clinical Center, National Institutes of Health, Bethesda, Maryland 20892-1590, USA. mossj@nhlbi.nih.gov
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MeSH Terms
Descriptor/Qualifier:
Adult
Forced Expiratory Volume
Humans
Lung Neoplasms / epidemiology*,  genetics*,  physiopathology,  radiography
Lymphangioleiomyomatosis / epidemiology*,  genetics*,  physiopathology,  radiography
Mass Screening
Population Surveillance
Prevalence
Prospective Studies
Registries
Respiratory Function Tests
Severity of Illness Index
Smoking / adverse effects
Tomography, X-Ray Computed
Tuberous Sclerosis / complications*
United States / epidemiology

From MEDLINE®/PubMed®, a database of the U.S. National Library of Medicine


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