Document Detail


Postpartum "psychosis" in mild argininosuccinate synthetase deficiency.
MedLine Citation:
PMID:  15863597     Owner:  NLM     Status:  MEDLINE    
Abstract/OtherAbstract:
BACKGROUND: Urea cycle disorders are relatively rare but well-established causes of postpartum coma and death. Such clinical presentations have been reported previously in ornithine transcarbamylase and carbamyl phosphate synthetase deficiencies. CASE: We describe a woman, without prior symptoms of metabolic disease, who presented with hyperammonemia and psychiatric symptoms in the postpartum period. Initial diagnoses included acute fatty liver of pregnancy and postpartum psychosis. She was later found to have argininosuccinate synthetase deficiency after further metabolic investigations. Rare heterozygous mutations in the argininosuccinate synthetase gene were identified. CONCLUSION: Urea cycle disorders may present initially with postpartum psychiatric symptoms and may represent an underrecognized cause of "postpartum psychosis." We recommend obtaining metabolic studies in women with neurologic or severe psychiatric symptoms in the postpartum period.
Authors:
Gregory M Enns; William E O'Brien; Keiko Kobayashi; Haruhide Shinzawa; Joan E Pellegrino
Related Documents :
21688037 - Multiple laparotomic myomectomy during pregnancy: a case report.
22155197 - Pregnancy and vasculitis: a systematic review of the literature.
8525147 - Renal reserve in pregnancy.
21675877 - The role of oxidative stress in the pathophysiology of gestational diabetes mellitus.
18032047 - The internal control group in a register of antiepileptic drug use in pregnancy.
21220157 - Longitudinal study of the renin angiotensin aldosterone system in purebred spanish broo...
Publication Detail:
Type:  Case Reports; Journal Article    
Journal Detail:
Title:  Obstetrics and gynecology     Volume:  105     ISSN:  0029-7844     ISO Abbreviation:  Obstet Gynecol     Publication Date:  2005 May 
Date Detail:
Created Date:  2005-05-02     Completed Date:  2005-06-30     Revised Date:  2009-10-26    
Medline Journal Info:
Nlm Unique ID:  0401101     Medline TA:  Obstet Gynecol     Country:  United States    
Other Details:
Languages:  eng     Pagination:  1244-6     Citation Subset:  AIM; IM    
Affiliation:
Division of Medical Genetics, Department of Pediatrics, Stanford University, Stanford, California 94305-5208, USA. greg.enns@stanford.edu
Export Citation:
APA/MLA Format     Download EndNote     Download BibTex
MeSH Terms
Descriptor/Qualifier:
Adult
Argininosuccinate Synthase / deficiency*
Depression, Postpartum / diagnosis*,  enzymology,  therapy
Diagnosis, Differential
Female
Follow-Up Studies
Humans
Metabolic Diseases / diagnosis*,  therapy
Postpartum Period
Pregnancy
Puerperal Disorders / diagnosis,  enzymology,  therapy
Risk Factors
Severity of Illness Index
Chemical
Reg. No./Substance:
EC 6.3.4.5/Argininosuccinate Synthase

From MEDLINE®/PubMed®, a database of the U.S. National Library of Medicine


Previous Document:  Herpes simplex virus 2-associated hemophagocytic lymphohistiocytosis in a pregnant patient.
Next Document:  Conservative management of placenta previa percreta in a Jehovah's Witness.