Document Detail


Plasma non-cholesterol sterols: a useful diagnostic tool in pediatric hypercholesterolemia.
MedLine Citation:
PMID:  20091938     Owner:  NLM     Status:  MEDLINE    
Abstract/OtherAbstract:
Current guidelines strongly recommend the identification of genetic forms of hypercholesterolemia (HC) during childhood.The usefulness of non-cholesterol sterols (NCS) in the diagnosis of genetic HC has not been fully explored. Plasma NCS were measured by gas chromatography/mass spectrometry (GC/MS) in 113 children with hypercholesterolemia affected by: autosomal dominant hypercholesterolemia (ADH), familial combined hyperlipidemia(FCHL), polygenic hypercholesterolemia (PHC), and in 79 controls to evaluate: i) plasma NCS profile in different genetic HC and ii) the usefulness of NCS for the diagnosis of HC beyond current clinical criteria. ADH was characterized by raised lathosterol/total cholesterol (TC) and reduced phytosterols/TC ratios, indicative of increased cholesterol synthesis. FCHL showed a slight increase of lathosterol/TC ratio, whereas PHC showed increased phytosterols/TC ratios, indicative of increased cholesterol absorption. In a post hoc discriminant analysis of patients with HC, lipid values correctly classified the 73% (14 of 19) of ADH, whereas the inclusion of plasma sterols allowed the correct identification of all 19 patients with ADH. FCHL was not differentiated from PHC (62 versus 69%).In conclusion, NCS measurement showed that cholesterol plasma levels are related to the cholesterol synthesis in ADH and to cholesterol absorption in PHC. NCS improve the detection of ADH in pediatric patients, whereas FCHL diagnosis is not improved.
Authors:
Davide Noto; Angelo B Cefal?; Giacoma Barraco; Eliana Martino; Francesca Fayer; Mariangela Min?; Anna Montali; Marcello Arca; Maurizio Averna; Francesco Martino
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Publication Detail:
Type:  Journal Article; Multicenter Study    
Journal Detail:
Title:  Pediatric research     Volume:  67     ISSN:  1530-0447     ISO Abbreviation:  Pediatr. Res.     Publication Date:  2010 Feb 
Date Detail:
Created Date:  2010-01-20     Completed Date:  2010-02-22     Revised Date:  -    
Medline Journal Info:
Nlm Unique ID:  0100714     Medline TA:  Pediatr Res     Country:  United States    
Other Details:
Languages:  eng     Pagination:  200-4     Citation Subset:  IM    
Affiliation:
Department of Clinical Medicine and Emerging Diseases, University of Palermo, Palermo I90127, Italy.
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MeSH Terms
Descriptor/Qualifier:
Adolescent
Biological Markers / blood
Case-Control Studies
Child
Cholesterol / analogs & derivatives,  blood
Discriminant Analysis
Female
Gas Chromatography-Mass Spectrometry
Genetic Predisposition to Disease
Humans
Hyperlipidemia, Familial Combined / blood,  diagnosis*,  genetics
Hyperlipoproteinemia Type II / blood,  diagnosis*,  genetics
Italy
Male
Multifactorial Inheritance
Phytosterols / blood
Predictive Value of Tests
Sitosterols / blood
Sterols / blood*
Chemical
Reg. No./Substance:
0/Biological Markers; 0/Phytosterols; 0/Sitosterols; 0/Sterols; 474-62-4/campesterol; 57-88-5/Cholesterol; 5779-62-4/sitosterol; 80-99-9/lathosterol

From MEDLINE®/PubMed®, a database of the U.S. National Library of Medicine


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