Document Detail


Perry syndrome due to the DCTN1 G71R mutation: a distinctive levodopa responsive disorder with behavioral syndrome, vertical gaze palsy, and respiratory failure.
MedLine Citation:
PMID:  20437543     Owner:  NLM     Status:  MEDLINE    
Abstract/OtherAbstract:
Perry syndrome is a rare form of autosomal dominant Parkinsonism with respiratory failure recently defined as being due to mutations in the DCTN1 gene. We describe a new family carrying a G71R mutation in the DCTN1 gene. The proband displayed a series of distinctive features not previously described in Perry syndrome: a disorder of vertical downward saccades accompanied by progressive midbrain atrophy, predominant nonmotor symptoms responsive to levodopa, distinctive craniocervical levodopa induced dyskinesias, and a good response to high-dose levodopa therapy and respiratory support. The family was initially thought to have autosomal dominant behavioral variant frontotemporal dementia with Parkinsonism. This report expands the clinical definition of this distinctive syndrome.
Authors:
Victoria Newsway; Mark Fish; Jonathan D Rohrer; Elisa Majounie; Nigel Williams; Melissa Hack; Jason D Warren; Huw R Morris
Related Documents :
16424003 - Pten autoregulates its expression by stabilization of p53 in a phosphatase-independent ...
17875913 - Clinical characterization of the hoxa1 syndrome bsas variant.
2486013 - The superior mesenteric artery syndrome: an unusual complication in a patient with the ...
Publication Detail:
Type:  Case Reports; Journal Article; Research Support, Non-U.S. Gov't    
Journal Detail:
Title:  Movement disorders : official journal of the Movement Disorder Society     Volume:  25     ISSN:  1531-8257     ISO Abbreviation:  Mov. Disord.     Publication Date:  2010 Apr 
Date Detail:
Created Date:  2010-05-03     Completed Date:  2010-07-28     Revised Date:  2011-07-18    
Medline Journal Info:
Nlm Unique ID:  8610688     Medline TA:  Mov Disord     Country:  United States    
Other Details:
Languages:  eng     Pagination:  767-70     Citation Subset:  IM    
Copyright Information:
2009 Movement Disorder Society
Affiliation:
MRC Centre for Neuropsychatric Genetics and Genomics, Cardiff University School of Medicine, Cardiff, United Kingdom.
Export Citation:
APA/MLA Format     Download EndNote     Download BibTex
MeSH Terms
Descriptor/Qualifier:
Arginine / genetics
Behavioral Symptoms / complications,  drug therapy,  genetics*
DNA Mutational Analysis
Dopamine Agents / therapeutic use
Glycine / genetics
Humans
Levodopa / therapeutic use
Male
Microtubule-Associated Proteins / genetics*
Middle Aged
Neuropsychological Tests
Optic Nerve Diseases / complications,  drug therapy,  genetics*
Parkinsonian Disorders / complications,  drug therapy,  genetics*
Respiratory Insufficiency / complications,  drug therapy,  genetics*
Grant Support
ID/Acronym/Agency:
//Medical Research Council; //Wellcome Trust
Chemical
Reg. No./Substance:
0/Dopamine Agents; 0/Levodopa; 0/Microtubule-Associated Proteins; 144198-36-7/dynactin; 56-40-6/Glycine; 74-79-3/Arginine

From MEDLINE®/PubMed®, a database of the U.S. National Library of Medicine


Previous Document:  The changing face of Parkinson's disease-associated psychosis: a cross-sectional study based on the ...
Next Document:  Sequencing analysis of the ITPR1 gene in a pure autosomal dominant spinocerebellar ataxia series.