Document Detail


Perlecan modulates VEGF signaling and is essential for vascularization in endochondral bone formation.
MedLine Citation:
PMID:  22421594     Owner:  NLM     Status:  MEDLINE    
Abstract/OtherAbstract:
Perlecan (Hspg2) is a heparan sulfate proteoglycan expressed in basement membranes and cartilage. Perlecan deficiency (Hspg2(-/-)) in mice and humans causes lethal chondrodysplasia, which indicates that perlecan is essential for cartilage development. However, the function of perlecan in endochondral ossification is not clear. Here, we report the critical role of perlecan in VEGF signaling and angiogenesis in growth plate formation. The Hspg2(-/-) growth plate was significantly wider but shorter due to severely impaired endochondral bone formation. Hypertrophic chondrocytes were differentiated in Hspg2(-/-) growth plates; however, removal of the hypertrophic matrix and calcified cartilage was inhibited. Although the expression of MMP-13, CTGF, and VEGFA was significantly upregulated in Hspg2(-/-) growth plates, vascular invasion into the hypertrophic zone was impaired, which resulted in an almost complete lack of bone marrow and trabecular bone. We demonstrated that cartilage perlecan promoted activation of VEGF/VEGFR by binding to the VEGFR of endothelial cells. Expression of the perlecan transgene specific to the cartilage of Hspg2(-/-) mice rescued their perinatal lethality and growth plate abnormalities, and vascularization into the growth plate was restored, indicating that perlecan in the growth plate, not in endothelial cells, is critical in this process. These results suggest that perlecan in cartilage is required for activating VEGFR signaling of endothelial cells for vascular invasion and for osteoblast migration into the growth plate. Thus, perlecan in cartilage plays a critical role in endochondral bone formation by promoting angiogenesis essential for cartilage matrix remodeling and subsequent endochondral bone formation.
Authors:
Muneaki Ishijima; Nobuharu Suzuki; Kentaro Hozumi; Tomoya Matsunobu; Keisuke Kosaki; Haruka Kaneko; John R Hassell; Eri Arikawa-Hirasawa; Yoshihiko Yamada
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Publication Detail:
Type:  Journal Article; Research Support, N.I.H., Intramural; Research Support, Non-U.S. Gov't     Date:  2012-03-07
Journal Detail:
Title:  Matrix biology : journal of the International Society for Matrix Biology     Volume:  31     ISSN:  1569-1802     ISO Abbreviation:  Matrix Biol.     Publication Date:  2012 May 
Date Detail:
Created Date:  2012-04-30     Completed Date:  2012-08-13     Revised Date:  2013-05-03    
Medline Journal Info:
Nlm Unique ID:  9432592     Medline TA:  Matrix Biol     Country:  Netherlands    
Other Details:
Languages:  eng     Pagination:  234-45     Citation Subset:  IM    
Copyright Information:
Published by Elsevier B.V.
Affiliation:
Laboratory of Cell and Developmental Biology, National Institute of Dental and Craniofacial Research, National Institutes of Health, Bethesda, Maryland 20892-4370, USA.
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MeSH Terms
Descriptor/Qualifier:
Animals
Basement Membrane / metabolism
Bone Marrow / metabolism,  pathology
Cartilage / metabolism,  pathology
Cell Differentiation
Cell Movement
Chondrocytes / metabolism,  pathology
Embryo, Mammalian / embryology,  metabolism
Endothelial Cells / metabolism,  pathology
Growth Plate / metabolism,  pathology
Heparan Sulfate Proteoglycans / genetics,  metabolism*
Hypertrophy / metabolism
Matrix Metalloproteinase 13 / genetics,  metabolism
Mice
Mice, Knockout
Mice, Transgenic / genetics,  metabolism
Neovascularization, Pathologic / metabolism*
Osteoblasts / metabolism
Osteogenesis*
Signal Transduction*
Transgenes
Vascular Endothelial Growth Factor A / metabolism*
Grant Support
ID/Acronym/Agency:
ZIA DE000483-21/DE/NIDCR NIH HHS; ZIA DE000483-22/DE/NIDCR NIH HHS; ZIA DE000483-23/DE/NIDCR NIH HHS; ZIA DE000720-03/DE/NIDCR NIH HHS; ZIA DE000720-04/DE/NIDCR NIH HHS; ZIA DE000720-05/DE/NIDCR NIH HHS
Chemical
Reg. No./Substance:
0/Heparan Sulfate Proteoglycans; 0/Vascular Endothelial Growth Factor A; 0/vascular endothelial growth factor A, mouse; 143972-95-6/perlecan; EC 3.4.24.-/Matrix Metalloproteinase 13; EC 3.4.24.-/Mmp13 protein, mouse

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