Document Detail


Pediatric writer's cramp in myoclonus-dystonia: maternal imprinting hides positive family history.
MedLine Citation:
PMID:  18571946     Owner:  NLM     Status:  MEDLINE    
Abstract/OtherAbstract:
Myoclonus-dystonia (M-D) is an autosomal dominantly inherited movement disorder with myoclonic jerks and dystonic contractions most frequently due to a mutation in the epsilon-sarcoglycan (SGCE, DYT11) gene. We describe two unrelated children with M-D (DYT11) who presented with writer's cramp. Due to maternal imprinting the family history appeared initially negative for M-D. In children with writer's cramp screening of the SGCE gene should be considered, even with a negative family history.
Authors:
M C F Gerrits; E M J Foncke; J H T M Koelman; M A J Tijssen
Publication Detail:
Type:  Case Reports; Journal Article; Research Support, Non-U.S. Gov't     Date:  2008-06-20
Journal Detail:
Title:  European journal of paediatric neurology : EJPN : official journal of the European Paediatric Neurology Society     Volume:  13     ISSN:  1532-2130     ISO Abbreviation:  Eur. J. Paediatr. Neurol.     Publication Date:  2009 Mar 
Date Detail:
Created Date:  2009-03-02     Completed Date:  2009-05-13     Revised Date:  -    
Medline Journal Info:
Nlm Unique ID:  9715169     Medline TA:  Eur J Paediatr Neurol     Country:  England    
Other Details:
Languages:  eng     Pagination:  178-80     Citation Subset:  IM    
Affiliation:
Department of Neurology, Academic Medical Centre, University of Amsterdam, The Netherlands. mignongerrits@hotmail.com
Export Citation:
APA/MLA Format     Download EndNote     Download BibTex
MeSH Terms
Descriptor/Qualifier:
Child
Dystonic Disorders / diagnosis*,  genetics*,  physiopathology
Family Health
Genomic Imprinting
Humans
Male
Mutation
Myoclonus / diagnosis*,  genetics*,  physiopathology
Pedigree
Sarcoglycans / genetics*
Chemical
Reg. No./Substance:
0/Sarcoglycans

From MEDLINE®/PubMed®, a database of the U.S. National Library of Medicine


Previous Document:  Congenital thenar hypoplasia with absent radial artery - a case report.
Next Document:  Development of vestibular evoked myogenic potentials in early life.