Document Detail


Ocular motor indicators of executive dysfunction in fragile X and Turner syndromes.
MedLine Citation:
PMID:  17107741     Owner:  NLM     Status:  MEDLINE    
Abstract/OtherAbstract:
Fragile X and Turner syndromes are two X-chromosome-related disorders associated with executive function and visual spatial deficits. In the present study, we used ocular motor paradigms to examine evidence that disruption to different neurological pathways underlies these deficits. We tested 17 females with fragile X, 19 females with Turner syndrome, and 40 females with neither disorder who comprised the comparison group. Group differences emerged for both the fragile X and Turner syndrome groups, each relative to the comparison group: Females with fragile X had deficits in generating memory-guided saccades, predictive saccades, and saccades made in the overlap condition of a gap/overlap task. Females with Turner syndrome showed deficits in generating memory-guided saccades, but not during either the predictive saccade or gap/overlap task. Females with Turner syndrome, but not females with fragile X, showed deficits in visually guided saccades and anti-saccades. These findings indicate that different brain regions are affected in the two disorders, and suggest that different pathways lead to the similar cognitive phenotypes described for fragile X and Turner syndromes.
Authors:
Adrian G Lasker; Michèle M M Mazzocco; David S Zee
Publication Detail:
Type:  Comparative Study; Journal Article; Research Support, N.I.H., Extramural     Date:  2006-11-14
Journal Detail:
Title:  Brain and cognition     Volume:  63     ISSN:  0278-2626     ISO Abbreviation:  Brain Cogn     Publication Date:  2007 Apr 
Date Detail:
Created Date:  2007-03-13     Completed Date:  2007-05-10     Revised Date:  2007-12-03    
Medline Journal Info:
Nlm Unique ID:  8218014     Medline TA:  Brain Cogn     Country:  United States    
Other Details:
Languages:  eng     Pagination:  203-20     Citation Subset:  IM    
Affiliation:
Department of Neurology, Suite 2210, Pathology Building, The Johns Hopkins School of Medicine, 601 N. Broadway, Baltimore, MD 21287-6921, USA. alasker@dizzy.med.jhu.edu
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MeSH Terms
Descriptor/Qualifier:
Adolescent
Adult
Analysis of Variance
Child
Cognition Disorders / complications,  diagnosis*
Eye Movement Measurements
Female
Fragile X Syndrome / complications*,  physiopathology
Humans
Oculomotor Muscles / physiology,  physiopathology
Perceptual Disorders / complications,  diagnosis*
Reaction Time / physiology
Reference Values
Saccades / physiology*
Space Perception / physiology
Statistics, Nonparametric
Turner Syndrome / complications*,  physiopathology
Grant Support
ID/Acronym/Agency:
NS 35356/NS/NINDS NIH HHS; R01 HD 34061/HD/NICHD NIH HHS

From MEDLINE®/PubMed®, a database of the U.S. National Library of Medicine


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