Document Detail


Novel polymorphism in the FMR1 gene resulting in a "pseudodeletion" of FMR1 in a commonly used fragile X assay.
MedLine Citation:
PMID:  11229516     Owner:  NLM     Status:  MEDLINE    
Abstract/OtherAbstract:
The fragile X syndrome is the most commonly inherited cause of mental retardation. Genetic diagnosis of this disease relies on the detection of triplet repeat expansion in the FMR1 gene on the X chromosome. Although the majority of disease in fragile X patients is due to mutations involving triplet repeat expansion, deletion of various portions of FMR1 has also been described in association with the fragile X syndrome. Here we describe a rare polymorphism in the noncoding region of FMR1 that mimics detection of a deletion in a commonly used assay for fragile X syndrome, which can result in misdiagnosis of the disease.
Authors:
T M Daly; A Rafii; R A Martin; B A Zehnbauer
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Publication Detail:
Type:  Journal Article    
Journal Detail:
Title:  The Journal of molecular diagnostics : JMD     Volume:  2     ISSN:  1525-1578     ISO Abbreviation:  J Mol Diagn     Publication Date:  2000 Aug 
Date Detail:
Created Date:  2001-03-02     Completed Date:  2001-03-22     Revised Date:  2009-11-18    
Medline Journal Info:
Nlm Unique ID:  100893612     Medline TA:  J Mol Diagn     Country:  United States    
Other Details:
Languages:  eng     Pagination:  128-31     Citation Subset:  IM    
Affiliation:
Department of Pathology, Washington University School of Medicine and St Louis Children's Hospital, Missouri 63110, USA.
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MeSH Terms
Descriptor/Qualifier:
Artifacts
Base Sequence
Blotting, Southern
Deoxyribonuclease EcoRI / metabolism
Diagnostic Errors*
Fragile X Mental Retardation Protein
Fragile X Syndrome / diagnosis*,  genetics*
Gene Frequency
Humans
Male
Nerve Tissue Proteins / genetics*
Polymerase Chain Reaction
Polymorphism, Genetic*
Polymorphism, Restriction Fragment Length
RNA-Binding Proteins*
Sequence Analysis, DNA
Sequence Deletion / genetics*
Chemical
Reg. No./Substance:
0/FMR1 protein, human; 0/Nerve Tissue Proteins; 0/RNA-Binding Proteins; 139135-51-6/Fragile X Mental Retardation Protein; EC 3.1.21.-/Deoxyribonuclease EcoRI
Comments/Corrections

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