Document Detail


Neuropathy as a presenting feature in fragile X-associated tremor/ataxia syndrome.
MedLine Citation:
PMID:  17726686     Owner:  NLM     Status:  MEDLINE    
Abstract/OtherAbstract:
Peripheral neuropathy is common among patients with fragile X-associated tremor ataxia syndrome (FXTAS). Four patients with FXTAS are described with neuropathy as the presenting feature, two having received a prior diagnosis of Charcot-Marie-Tooth (CMT) disease. A fifth is described with neuropathy as the only clinical feature. A functional connection between FXTAS and neuropathy has been suggested by the presence of lamin A/C in the intranuclear, neuronal and astrocytic inclusions of FXTAS, since mutations in lamin A/C are known to give rise to an axonal form of CMT.
Authors:
Randi J Hagerman; Sarah M Coffey; Ricardo Maselli; Kultida Soontarapornchai; James A Brunberg; Maureen A Leehey; Lin Zhang; Louise W Gane; Grace Fenton-Farrell; Flora Tassone; Paul J Hagerman
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Publication Detail:
Type:  Case Reports; Journal Article; Research Support, N.I.H., Extramural; Research Support, Non-U.S. Gov't    
Journal Detail:
Title:  American journal of medical genetics. Part A     Volume:  143A     ISSN:  1552-4825     ISO Abbreviation:  Am. J. Med. Genet. A     Publication Date:  2007 Oct 
Date Detail:
Created Date:  2007-10-01     Completed Date:  2008-01-15     Revised Date:  2008-05-21    
Medline Journal Info:
Nlm Unique ID:  101235741     Medline TA:  Am J Med Genet A     Country:  United States    
Other Details:
Languages:  eng     Pagination:  2256-60     Citation Subset:  IM    
Copyright Information:
2007 Wiley-Liss, Inc
Affiliation:
Department of Pediatrics, University of California at Davis Medical Center, Sacramento, California 95817, USA. randi.hagerman@ucdmc.ucdavis.edu
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MeSH Terms
Descriptor/Qualifier:
Aged
Ataxia / complications,  physiopathology
Female
Fragile X Syndrome / complications,  physiopathology*
Humans
Male
Middle Aged
Peripheral Nervous System Diseases / complications*
Tremor / complications,  physiopathology
Grant Support
ID/Acronym/Agency:
AG24488/AG/NIA NIH HHS; HD02274/HD/NICHD NIH HHS; HD036071/HD/NICHD NIH HHS; NS044299/NS/NINDS NIH HHS

From MEDLINE®/PubMed®, a database of the U.S. National Library of Medicine


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