Document Detail


Multiple facial milia in patients with loeys-dietz syndrome.
MedLine Citation:
PMID:  20956634     Owner:  NLM     Status:  In-Data-Review    
Abstract/OtherAbstract:
BACKGROUND: Loeys-Dietz syndrome (LDS) results from mutations in the TGFBR1 or TGFBR2 genes and is known to cause aggressive cardiovascular disease, including aortic aneurysms and dissections at an early age. Currently, craniofacial, skeletal, and cardiovascular findings play an important role in early recognition of the disease. While many patients do have recognizable cutaneous features of LDS, little information about associated skin findings has been reported.
OBSERVATIONS: Four unrelated patients with LDS due to a mutation in the TGFBR2 gene were observed to have numerous facial milia. All 4 patients reported that the milia had been present since early childhood and had increased in number with time. In some cases, affected relatives were reported to have similar findings.
CONCLUSIONS: To our knowledge, the association of LDS and facial milia has not been previously reported. Recognition of LDS is important because the aggressive aortic and arterial disease warrants early surgical therapy. Facial milia and other cutaneous findings may possibly differentiate LDS from Marfan syndrome and other related disorders, thereby facilitating early diagnosis. Interestingly, each of the 4 patients with LDS and facial milia had a mutation in TGFBR2 despite widespread variability in other features of the disease.
Authors:
Brendan M Lloyd; Alan C Braverman; Milan J Anadkat
Related Documents :
17570934 - Alport syndrome and thin basement membrane nephropathy.
15734684 - Genetic modulation of senescent phenotypes in homo sapiens.
12020474 - Diseases of the neuromuscular junction.
16028794 - Audiological and vestibular features in affected subjects with ush3: a genotype/phenoty...
12484714 - Novel insights in the congenital long qt syndrome.
15171814 - Immunological features of neurological paraneoplastic syndromes.
Publication Detail:
Type:  Journal Article     Date:  2010-10-18
Journal Detail:
Title:  Archives of dermatology     Volume:  147     ISSN:  1538-3652     ISO Abbreviation:  Arch Dermatol     Publication Date:  2011 Feb 
Date Detail:
Created Date:  2011-02-22     Completed Date:  -     Revised Date:  -    
Medline Journal Info:
Nlm Unique ID:  0372433     Medline TA:  Arch Dermatol     Country:  United States    
Other Details:
Languages:  eng     Pagination:  223-6     Citation Subset:  AIM; IM    
Affiliation:
Division of Dermatology, Washington University School of Medicine, 4921 Parkview Pl, Ste 5B, St Louis, MO 63110. manadkat@dom.wustl.edu.
Export Citation:
APA/MLA Format     Download EndNote     Download BibTex
MeSH Terms
Descriptor/Qualifier:

From MEDLINE®/PubMed®, a database of the U.S. National Library of Medicine


Previous Document:  The Performance of MelaFind: A Prospective Multicenter Study.
Next Document:  A Randomized Comparison of Methods of Selecting Narrowband UV-B Starting Dose to Treat Chronic Psori...