Document Detail


Membranous nephropathy in Schimke immuno-osseous dysplasia.
MedLine Citation:
PMID:  16570201     Owner:  NLM     Status:  MEDLINE    
Abstract/OtherAbstract:
Schimke immuno-osseous dysplasia is a rare autosomal recessive multi-system disorder, with clinical features of growth retardation, spondylo-epiphyseal dysplasia, nephrotic syndrome and immunodeficiency beginning in childhood. Here, we report a new case, in a 10-year-old boy with characteristic symptoms of Schimke immuno-osseous dysplasia. The patient presented with short stature and, later, developed nephrotic syndrome and peritonitis. In addition, he had perinuclear anti-neutrophilic cytoplasmic antibody (p-ANCA)-positive arthritis. Renal pathology of the patients with this disease usually show focal segmental glomerulonephritis, whereas our patient had membranous nephropathy, which has not previously been reported.
Authors:
Nihal Ozdemir; Harika Alpay; Abdullah Bereket; Gamze Bereket; Neşe Biyikli; Metin Aydoğan; Fulya Cakalağoğlu; Işin Kiliçaslan; Ihsan Akpinar
Publication Detail:
Type:  Case Reports; Journal Article     Date:  2006-03-29
Journal Detail:
Title:  Pediatric nephrology (Berlin, Germany)     Volume:  21     ISSN:  0931-041X     ISO Abbreviation:  Pediatr. Nephrol.     Publication Date:  2006 Jun 
Date Detail:
Created Date:  2006-05-16     Completed Date:  2006-11-14     Revised Date:  -    
Medline Journal Info:
Nlm Unique ID:  8708728     Medline TA:  Pediatr Nephrol     Country:  Germany    
Other Details:
Languages:  eng     Pagination:  870-2     Citation Subset:  IM    
Affiliation:
Paediatric Nephrology, Marmara University, Istanbul, Turkey.
Export Citation:
APA/MLA Format     Download EndNote     Download BibTex
MeSH Terms
Descriptor/Qualifier:
Abnormalities, Multiple / diagnosis
Child
Face / abnormalities
Glomerulonephritis, Membranous / diagnosis*,  pathology
Growth Disorders / diagnosis*
Humans
Immunologic Deficiency Syndromes / diagnosis*
Male
Osteochondrodysplasias / diagnosis*
Syndrome

From MEDLINE®/PubMed®, a database of the U.S. National Library of Medicine


Previous Document:  Genome-wide linkage analysis of population variation in high-density lipoprotein cholesterol.
Next Document:  Renal amyloidosis in a child with sickle cell anemia.