Document Detail


Long-term outcomes of adults with features of VACTERL association.
MedLine Citation:
PMID:  20888933     Owner:  NLM     Status:  MEDLINE    
Abstract/OtherAbstract:
VACTERL association involves the presence of specific congenital, multi-organ malformations that tend to co-occur. Clinical and research efforts typically center on pediatric patients, and there is a scarcity of information in the literature regarding VACTERL-related issues and outcomes in adulthood. We describe here 11 adults with features of VACTERL association ascertained through our research study on the condition. In our cohort of adult patients, approximately 25% of medically significant malformations that are component features of VACTERL association, including 40% of vertebral, 50% of cardiac, and 50% of renal anomalies, were not identified during childhood. Additionally, medical sequelae of many of the primary malformations identified in infancy or early childhood persist or are first reported in adulthood. These sequelae can involve challenging medical and surgical management in adulthood. As most adults with VACTERL association are not specifically followed for VACTERL-related issues, a more uniform diagnostic work-up and a low threshold for investigation of medical sequelae of the primary disorder may enhance the quality of clinical management in these patients.
Authors:
Manu S Raam; Daniel E Pineda-Alvarez; Donald W Hadley; Benjamin D Solomon
Related Documents :
15734013 - Medication use and retinal vessel diameters.
17291673 - Hyperventilation following aero-medical rapid sequence intubation may be a deliberate r...
11828833 - Co-prescribing of medications used to treat obstructive lung disease, congestive heart ...
Publication Detail:
Type:  Case Reports; Journal Article; Research Support, N.I.H., Intramural; Research Support, Non-U.S. Gov't     Date:  2010-10-01
Journal Detail:
Title:  European journal of medical genetics     Volume:  54     ISSN:  1878-0849     ISO Abbreviation:  Eur J Med Genet     Publication Date:    2011 Jan-Feb
Date Detail:
Created Date:  2011-02-28     Completed Date:  2011-06-14     Revised Date:  2012-01-04    
Medline Journal Info:
Nlm Unique ID:  101247089     Medline TA:  Eur J Med Genet     Country:  Netherlands    
Other Details:
Languages:  eng     Pagination:  34-41     Citation Subset:  IM    
Copyright Information:
Published by Elsevier Masson SAS.
Affiliation:
Medical Genetics Branch, National Human Genome Research Institute, National Institutes of Health, Building 35, Room 1B207, 35 Convent Drive MSC 3717, Bethesda, MD 20892-3717, USA. raamm@ccf.org
Export Citation:
APA/MLA Format     Download EndNote     Download BibTex
MeSH Terms
Descriptor/Qualifier:
Abnormalities, Multiple / pathology*
Adult
Anal Canal / abnormalities*
Cohort Studies
Esophagus / abnormalities*
Female
Heart Defects, Congenital / pathology*
Humans
Kidney / abnormalities*
Limb Deformities, Congenital / pathology
Male
Middle Aged
Spine / abnormalities*
Time Factors
Trachea / abnormalities
Grant Support
ID/Acronym/Agency:
Z99 HG999999/HG/NHGRI NIH HHS; //Howard Hughes Medical Institute

From MEDLINE®/PubMed®, a database of the U.S. National Library of Medicine


Previous Document:  Neuropathy in Wolfram syndrome.
Next Document:  de novo RYR1 heterozygous mutation (I4898T) causing lethal core-rod myopathy in twins.