Document Detail


Kindler syndrome.
MedLine Citation:
PMID:  19945624     Owner:  NLM     Status:  MEDLINE    
Abstract/OtherAbstract:
Kindler syndrome (MIM173650) is an autosomal recessive genodermatosis characterized by poikiloderma, trauma-induced skin blistering, mucosal inflammation, and photosensitivity. Loss-of-function mutations in the FERMT1 gene are the cause of Kindler syndrome. Kindler syndrome is categorized as a subtype of epidermolysis bullosa (EB). During infancy and childhood, there is clinical overlap between Kindler syndrome and dystrophic EB. Unlike other forms of EB, Kindler syndrome is characterized by impaired actin cytoskeleton-extracellular matrix interactions and a variable plane of blister formation at or close to the dermal-epidermal junction. This article reviews clinicopathologic and molecular features of Kindler syndrome and discusses patient management.
Authors:
Joey E Lai-Cheong; John A McGrath
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Publication Detail:
Type:  Journal Article; Research Support, Non-U.S. Gov't; Review    
Journal Detail:
Title:  Dermatologic clinics     Volume:  28     ISSN:  1558-0520     ISO Abbreviation:  Dermatol Clin     Publication Date:  2010 Jan 
Date Detail:
Created Date:  2009-11-30     Completed Date:  2010-02-17     Revised Date:  -    
Medline Journal Info:
Nlm Unique ID:  8300886     Medline TA:  Dermatol Clin     Country:  United States    
Other Details:
Languages:  eng     Pagination:  119-24     Citation Subset:  IM    
Affiliation:
Division of Genetics and Molecular Medicine, St John's Institute of Dermatology, King's College London, Floor 9 Tower Wing, Guy's Hospital, Great Maze Pond, London SE1 9RT, UK.
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MeSH Terms
Descriptor/Qualifier:
Atrophy
Blister / metabolism,  pathology
Dermis / metabolism,  pathology*
Epidermis / metabolism,  pathology*
Epidermolysis Bullosa / metabolism,  pathology*,  therapy
Humans
Grant Support
ID/Acronym/Agency:
//Wellcome Trust

From MEDLINE®/PubMed®, a database of the U.S. National Library of Medicine


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