Document Detail


Involvement of PTCH gene in various noninflammatory cysts.
MedLine Citation:
PMID:  10868476     Owner:  NLM     Status:  MEDLINE    
Abstract/OtherAbstract:
Constitutional hemizygous inactivation of PTCH, the Shh signaling pathway gene that moderates the signal, manifests itself as nevoid basal cell carcinoma syndrome or Gorlin syndrome, a condition variably characterized by a number of developmental disorders and malformations, and by predisposition to some malignancies, basal cell carcinoma in particular. Loss of heterozygosity for the PTCH region was found several years ago in the epithelial lining of odontogenic keratocysts, the cyst type with highly increased incidence in nevoid basal cell carcinoma syndrome. This finding confirmed the expectations that the gene responsible for the syndrome would have a decisive role in the genesis of these cysts even when they are not syndrome related. Suggestive temporal distribution of Shh signaling, recently observed during tooth development, lead us to investigate PTCH association with dentigerous cysts, the other major noninflammatory cyst of odontogenic origin. We report here that PTCH appears to be inactivated in dentigerous cysts, suggesting that it is responsible for their genesis as well. More generally, if our similar observations of incomplete heterozygosity in this region for dermoid cysts can be interpreted as loss of heterozygosity, PTCH alterations may prove to be a necessary, and perhaps the initiating event, in formation and growth of various noninflammatory cysts. This would be consistent with our view that local PTCH inactivation can, under favorable circumstances, lead to persistent though not by itself truly aggressive cell proliferation.
Authors:
S Levanat; B Pavelić; I Crnić; S Oresković; S Manojlović
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Publication Detail:
Type:  Journal Article    
Journal Detail:
Title:  Journal of molecular medicine (Berlin, Germany)     Volume:  78     ISSN:  0946-2716     ISO Abbreviation:  J. Mol. Med.     Publication Date:  2000  
Date Detail:
Created Date:  2000-10-24     Completed Date:  2000-10-24     Revised Date:  2011-07-08    
Medline Journal Info:
Nlm Unique ID:  9504370     Medline TA:  J Mol Med (Berl)     Country:  GERMANY    
Other Details:
Languages:  eng     Pagination:  140-6     Citation Subset:  IM    
Affiliation:
Division of Molecular Medicine, Ruder Bosković Institute, Zagreb, Croatia. levanat@rudjer.irb.hr
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MeSH Terms
Descriptor/Qualifier:
Adolescent
Adult
Aged
Dentigerous Cyst / genetics*,  metabolism*
Female
Genetic Markers
Hedgehog Proteins
Humans
Jaw Diseases / genetics*,  metabolism*
Loss of Heterozygosity
Male
Membrane Proteins / genetics*,  metabolism*
Middle Aged
Ovarian Cysts / genetics,  metabolism
Polymerase Chain Reaction
Polymorphism, Genetic
Proteins / genetics,  metabolism
Receptors, Cell Surface
Sequence Analysis, DNA
Tooth / embryology,  metabolism
Trans-Activators*
Chemical
Reg. No./Substance:
0/Genetic Markers; 0/Hedgehog Proteins; 0/Membrane Proteins; 0/Proteins; 0/Receptors, Cell Surface; 0/SHH protein, human; 0/Trans-Activators; 0/patched receptors

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