Document Detail


Intrafamilial variability in fragile X-associated tremor/ataxia syndrome.
MedLine Citation:
PMID:  16124012     Owner:  NLM     Status:  MEDLINE    
Abstract/OtherAbstract:
Fragile X-associated tremor/ataxia syndrome (FXTAS) is a progressive adult-onset tremor/ataxia syndrome caused by premutations in the FMR1 gene. In cranial MRI, the most characteristic findings are bilateral T2 hyperintense lesions within the middle cerebellar peduncles. Here we present a sibpair of two affected brothers presenting with very different symptoms (typical FXTAS versus essential tremor-like), disease progression, and MRI findings, illustrating broad intrafamilial variability of FXTAS. Also, their family history suggests further evidence of possible manifestation of FXTAS in women.
Authors:
Nils Peters; Christoph Kamm; Friedrich Asmus; Elke Holinski-Feder; Eduard Kraft; Martin Dichgans; Roland Brüning; Thomas Gasser; Kai Bötzel
Publication Detail:
Type:  Case Reports; Journal Article    
Journal Detail:
Title:  Movement disorders : official journal of the Movement Disorder Society     Volume:  21     ISSN:  0885-3185     ISO Abbreviation:  Mov. Disord.     Publication Date:  2006 Jan 
Date Detail:
Created Date:  2006-01-19     Completed Date:  2006-07-03     Revised Date:  2008-11-21    
Medline Journal Info:
Nlm Unique ID:  8610688     Medline TA:  Mov Disord     Country:  United States    
Other Details:
Languages:  eng     Pagination:  98-102     Citation Subset:  IM    
Copyright Information:
Copyright (c) 2005 Movement Disorder Society.
Affiliation:
Department of Neurology, Klinikum Grosshadern, Ludwig Maximilians University Munich, Munich, Germany.
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MeSH Terms
Descriptor/Qualifier:
Atrophy
Cerebellum / pathology
DNA Mutational Analysis
Deep Brain Stimulation
Female
Follow-Up Studies
Fragile X Mental Retardation Protein / genetics*
Fragile X Syndrome / diagnosis,  genetics*,  therapy
Gait Apraxia / diagnosis,  genetics*,  therapy
Genetic Variation / genetics*
Humans
Magnetic Resonance Imaging
Male
Middle Aged
Neurologic Examination
Pedigree
Sex Factors
Spinocerebellar Degenerations / diagnosis,  genetics*,  therapy
Tremor / diagnosis,  genetics*,  therapy
Trinucleotide Repeats / genetics
Chemical
Reg. No./Substance:
0/FMR1 protein, human; 139135-51-6/Fragile X Mental Retardation Protein

From MEDLINE®/PubMed®, a database of the U.S. National Library of Medicine


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