Document Detail


In utero gene delivery by intraamniotic injection of a retroviral vector producer cell line in a nonhuman primate model.
MedLine Citation:
PMID:  11589828     Owner:  NLM     Status:  MEDLINE    
Abstract/OtherAbstract:
In utero gene therapy (IUGT) offers the promise of treating a wide variety of genetic diseases before the development of disease manifestations. The most convenient and potentially easiest method of targeting the fetus is through injection into the amniotic cavity. For long-term correction of genetic defects, retroviral vectors have great potential as a tool for gene therapy strategies. However, retroviral vectors are limited by growth to low titers. In an attempt to increase the amount of vector particles delivered and assess the potential of intraamniotic administration, we injected a retroviral vector producer cell line encoding the lacZ gene into the amniotic fluid of a nonhuman primate model. After birth the infants were analyzed for vector-mediated transduction. Two of four fetuses were successfully transduced, with transgene expression detected in the esophagus, trachea, and stomach. In some sections of tissue, nearly 100% of the cells lining the lumen of these tissues were positive for transduction. Although successful, the limited number of tissues in which transduction was observed led to an in vitro analysis of the effects of amniotic fluid (AF). The presence of amniotic fluid inhibited transduction by 99%. AF affected both the transducing activity of the vector and the health of the packaging cells. The negative effects of AF were gestational age dependent; greater inhibition was observed from AF collected at later stages of pregnancy. The fact that transduction was successful despite these negative effects indicates that this approach is a promising strategy for gene therapy.
Authors:
M Bennett; H Galan; G Owens; R Dewey; R Banks; J Hobbins; F Accurso; J Schaack
Related Documents :
1602818 - Gene therapy model for stromal precursor cells of hematopoietic microenvironment.
16713998 - Murine leukemia virus vector integration favors promoter regions and regional hot spots...
12428748 - Vascular adventitia is a suitable compartment to transplant transduced vascular smooth ...
9384658 - The use of cytokines to improve gene transfer to human hematopoietic stem cells.
20705668 - Phenotypic and physiological alterations by heterologous acylhomoserine lactone synthas...
15668728 - Correlating gene expression with chemical scaffolds of cytotoxic agents: ellipticines a...
Publication Detail:
Type:  Journal Article; Research Support, Non-U.S. Gov't; Research Support, U.S. Gov't, P.H.S.    
Journal Detail:
Title:  Human gene therapy     Volume:  12     ISSN:  1043-0342     ISO Abbreviation:  Hum. Gene Ther.     Publication Date:  2001 Oct 
Date Detail:
Created Date:  2001-10-08     Completed Date:  2001-12-07     Revised Date:  2007-11-14    
Medline Journal Info:
Nlm Unique ID:  9008950     Medline TA:  Hum Gene Ther     Country:  United States    
Other Details:
Languages:  eng     Pagination:  1857-65     Citation Subset:  IM    
Affiliation:
Department of Microbiology, School of Medicine, University of Colorado Health Sciences Center, Denver, CO 80262, USA.
Export Citation:
APA/MLA Format     Download EndNote     Download BibTex
MeSH Terms
Descriptor/Qualifier:
3T3 Cells
Amniotic Fluid*
Animals
Cell Line
Esophagus / embryology
Female
Galactosides / metabolism
Gene Transfer Techniques*
Genetic Vectors
Gestational Age
Immunohistochemistry
Indoles / metabolism
Lac Operon
Macaca
Mice
Polymerase Chain Reaction
Pregnancy
Retroviridae / genetics*
Stomach / embryology
Time Factors
Trachea / embryology
Transduction, Genetic
Transgenes
Grant Support
ID/Acronym/Agency:
1K12HD01271-01A1/HD/NICHD NIH HHS; R01 HL58344/HL/NHLBI NIH HHS
Chemical
Reg. No./Substance:
0/Galactosides; 0/Indoles; 7240-90-6/5-bromo-4-chloro-3-indolyl beta-galactoside

From MEDLINE®/PubMed®, a database of the U.S. National Library of Medicine


Previous Document:  High-efficiency gene transfer into rhesus macaque primary T lymphocytes by combining 32 degrees C ce...
Next Document:  Dendritic cells transduced with HSV-1 amplicons expressing prostate-specific antigen generate antitu...