Document Detail


Hypertrichosis in patients with SURF1 mutations.
MedLine Citation:
PMID:  16222681     Owner:  NLM     Status:  MEDLINE    
Abstract/OtherAbstract:
We present three patients with SURF1 mutations. In addition to Leigh syndrome all patients had hypertrichosis, a clinical sign that is not usually associated with Leigh syndrome. The hypertrichosis was not congenital and it was mainly distributed on the extremities and forehead. In addition to our three patients, we have identified five patients in the literature with hypertrichosis and Leigh syndrome due to SURF1 mutations. Since most patients had onset of hypertrichosis before the diagnosis of Leigh syndrome was made, we suggest that clinicians consider Leigh syndrome in patients with, for example, psychomotor retardation or other unspecific symptoms in combination with hypertrichosis.
Authors:
Elsebet Ostergaard; Irena Bradinova; Susanne Holst Ravn; Flemming Juul Hansen; Emil Simeonov; Ernst Christensen; Flemming Wibrand; Marianne Schwartz
Publication Detail:
Type:  Case Reports; Journal Article    
Journal Detail:
Title:  American journal of medical genetics. Part A     Volume:  138     ISSN:  1552-4825     ISO Abbreviation:  Am. J. Med. Genet. A     Publication Date:  2005 Nov 
Date Detail:
Created Date:  2005-10-26     Completed Date:  2006-03-28     Revised Date:  2006-11-15    
Medline Journal Info:
Nlm Unique ID:  101235741     Medline TA:  Am J Med Genet A     Country:  United States    
Other Details:
Languages:  eng     Pagination:  384-8     Citation Subset:  IM    
Copyright Information:
Copyright 2005 Wiley-Liss, Inc
Affiliation:
John F. Kennedy Institute, Glostrup, Denmark. els@kennedy.dk
Export Citation:
APA/MLA Format     Download EndNote     Download BibTex
MeSH Terms
Descriptor/Qualifier:
Female
Humans
Hypertrichosis / genetics*
Infant
Infant, Newborn
Leigh Disease / pathology
Male
Membrane Proteins
Mitochondrial Proteins
Mutation*
Proteins / genetics*
Chemical
Reg. No./Substance:
0/Membrane Proteins; 0/Mitochondrial Proteins; 0/Proteins; 0/Surf-1 protein

From MEDLINE®/PubMed®, a database of the U.S. National Library of Medicine


Previous Document:  A 72-year-old Danish puzzle resolved--comparative analysis of phenotypes in families with different-...
Next Document:  Medial temporal lobe dysgenesis in hypochondroplasia.