Document Detail


Gonadal and müllerian duct agenesis in a girl with 46,X,i(Xq).
MedLine Citation:
PMID:  6700887     Owner:  NLM     Status:  MEDLINE    
Abstract/OtherAbstract:
A unique case of gonadal agenesis and rudimentary müllerian duct development in association with a 46,X,i(Xq) karyotype is reported. The patient presented with short stature and subtle features of Turner syndrome. Endocrine evaluation revealed elevated gonadotropins and cytogenetic findings from both peripheral blood leukocytes and skin fibroblasts were consistent with a 46,X,i(Xq) karyotype. Laparoscopy revealed both uterus and gonads to be absent. Developmental failure of the müllerian system in association with gonadal agenesis in a patient with 46,X,i(Xq) has not been previously reported. The basis for müllerian duct regression in this patient remains unclear. Recommendations for treatment are made.
Authors:
F D De Leon; J H Hersh; J S Sanfilippo; K N Schikler; F F Yen
Related Documents :
6156667 - Central retinal vein occlusion in reye's syndrome.
1758777 - Reye's syndrome associated with acute myocarditis and fatal circulatory failure.
3924247 - Defects of metabolism of fatty acids in the sudden infant death syndrome.
21739107 - Juvenile myoclonic epilepsy presenting as a new daily persistent-like headache.
8214367 - Acute lymphoid leukemia associated with maffucci's syndrome.
22937347 - Suspected "t-cell-mediated" hypereosinophilic syndrome presenting with cerebral watersh...
Publication Detail:
Type:  Case Reports; Journal Article    
Journal Detail:
Title:  Obstetrics and gynecology     Volume:  63     ISSN:  0029-7844     ISO Abbreviation:  Obstet Gynecol     Publication Date:  1984 Mar 
Date Detail:
Created Date:  1984-03-27     Completed Date:  1984-03-27     Revised Date:  2009-10-26    
Medline Journal Info:
Nlm Unique ID:  0401101     Medline TA:  Obstet Gynecol     Country:  UNITED STATES    
Other Details:
Languages:  eng     Pagination:  81S-83S     Citation Subset:  AIM; IM    
Export Citation:
APA/MLA Format     Download EndNote     Download BibTex
MeSH Terms
Descriptor/Qualifier:
Cervix Uteri / abnormalities
Child
Female
Gonadal Dysgenesis / diagnosis*,  genetics,  pathology
Humans
Karyotyping
Mullerian Ducts / pathology*
Sex Chromosome Aberrations / diagnosis*
Turner Syndrome / diagnosis*
Uterus / abnormalities
X Chromosome*

From MEDLINE®/PubMed®, a database of the U.S. National Library of Medicine


Previous Document:  Endometriosis with ascites.
Next Document:  Adrenal hypofunction and trisomy 18.