Document Detail


Functional pulmonary atresia in a patient with neonatal Marfan syndrome caused by a c.3602G>A mutation in exon 29 of the FBN1 gene.
MedLine Citation:
PMID:  18388785     Owner:  NLM     Status:  MEDLINE    
Abstract/OtherAbstract:
Neonatal Marfan syndrome is a severe form of the syndrome mostly caused by de-novo mutations in the fibrillin-1 gene. We report a newborn with neonatal Marfan syndrome and functional pulmonary atresia who died from congestive heart failure on postnatal day 22 despite treatment. He had a mutation in exon 29 of the fibrillin-1 gene at position c.3602G>A. Functional pulmonary atresia may be a life-threatening cardiovascular manifestation of neonatal Marfan syndrome.
Authors:
Murat Derbent; Deniz Anuk; Aylin Tarcan; Birgül Varan; Berkan Gurakan; Kursad Tokel
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Publication Detail:
Type:  Case Reports; Journal Article    
Journal Detail:
Title:  Clinical dysmorphology     Volume:  17     ISSN:  0962-8827     ISO Abbreviation:  Clin. Dysmorphol.     Publication Date:  2008 Apr 
Date Detail:
Created Date:  2008-04-04     Completed Date:  2008-05-27     Revised Date:  -    
Medline Journal Info:
Nlm Unique ID:  9207893     Medline TA:  Clin Dysmorphol     Country:  England    
Other Details:
Languages:  eng     Pagination:  127-8     Citation Subset:  IM    
Affiliation:
Department of Pediatrics, Baskent University Faculty of Medicine, Ankara, Turkey. mderbent@baskent-ank.edu.tr
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MeSH Terms
Descriptor/Qualifier:
Fatal Outcome
Heart / physiopathology
Heart Failure / etiology,  physiopathology
Humans
Infant, Newborn
Male
Marfan Syndrome / complications,  genetics*,  pathology
Microfilament Proteins / genetics*
Mutation, Missense*
Pulmonary Atresia / complications*,  physiopathology
Chemical
Reg. No./Substance:
0/Microfilament Proteins; 0/fibrillin

From MEDLINE®/PubMed®, a database of the U.S. National Library of Medicine


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