Document Detail


Fucosidosis and anesthesia.
MedLine Citation:
PMID:  17768480     Owner:  NLM     Status:  MEDLINE    
Abstract/OtherAbstract:
Fucosidosis is a rare, autosomal recessive lysosomal storage disorder caused by a severe deficiency of a-L-fucosidase. Patients usually have some problems with glycoprotein storage in the brain and other organs, and some structural abnormalities that need special consideration in anesthesia. It has 2 types, the early onset or infantile, and the juvenile. Here we present an 8-year old girl with deformities in the maxillofacial region, with big tongue, small and retracted chin, saddle nose, and short neck that could not be extended, causing difficult intubation, and congenital cardiac problems requiring a special anesthetic strategy.
Authors:
Alireza E Soltani; Reza S Moharari; Reza Ghaffari; Hamid Zahedi; Mojgan Hajmahmoodi
Publication Detail:
Type:  Case Reports; Journal Article    
Journal Detail:
Title:  Saudi medical journal     Volume:  28     ISSN:  0379-5284     ISO Abbreviation:  Saudi Med J     Publication Date:  2007 Sep 
Date Detail:
Created Date:  2007-09-04     Completed Date:  2008-02-05     Revised Date:  2008-06-23    
Medline Journal Info:
Nlm Unique ID:  7909441     Medline TA:  Saudi Med J     Country:  Saudi Arabia    
Other Details:
Languages:  eng     Pagination:  1446-8     Citation Subset:  IM    
Affiliation:
Department of Anesthesia, Children Medical Center, University of Tehran, Tehran, Iran.
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MeSH Terms
Descriptor/Qualifier:
Anesthesia / methods*
Child
Female
Fucosidosis / pathology*,  surgery
Glaucoma / etiology,  surgery
Humans

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