Document Detail


Focal epilepsy resulting from a de novo SCN1A mutation.
MedLine Citation:
PMID:  18330841     Owner:  NLM     Status:  MEDLINE    
Abstract/OtherAbstract:
We found a DE NOVO missense mutation of the gene encoding the alpha1 subunit of the neuro-nal voltage-gated sodium channel, SCN1A, in a patient with repetitive focal seizures. At 5 months of age, the patient had a first seizure characterized by loss of consciousness and clonic convulsions in the left hand followed by secondary generalization lasting for 20 minutes in association with pyrexia. Although valproate was administered, she has had generalized seizures every month, mostly in association with elevated body temperature. Since 32 months of age, she also had a different type of seizure characterized by a fearful response followed by decreased consciousness, pallor, and salivation. Myoclonia or atypical absence seizures have never been observed until the last follow-up at 42 months of age. Genetic analysis showed a heterozygous missense mutation (c.5311A>T: I1771F) in the patient, which was not detected in her parents.
Authors:
A Okumura; H Kurahashi; S Hirose; N Okawa; K Watanabe
Publication Detail:
Type:  Case Reports; Journal Article    
Journal Detail:
Title:  Neuropediatrics     Volume:  38     ISSN:  0174-304X     ISO Abbreviation:  Neuropediatrics     Publication Date:  2007 Oct 
Date Detail:
Created Date:  2008-03-11     Completed Date:  2008-06-05     Revised Date:  -    
Medline Journal Info:
Nlm Unique ID:  8101187     Medline TA:  Neuropediatrics     Country:  Germany    
Other Details:
Languages:  eng     Pagination:  253-6     Citation Subset:  IM    
Affiliation:
Department of Pediatrics, Juntendo University School of Medicine, Tokyo, Japan. okumura@med.juntendo.ac.jp
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MeSH Terms
Descriptor/Qualifier:
Developmental Disabilities / diagnosis,  genetics
Epilepsies, Partial / diagnosis,  genetics*
Epilepsy, Generalized / diagnosis,  genetics
Exanthema Subitum / diagnosis
Female
Humans
Infant
Infant, Newborn
Mutation, Missense*
Nerve Tissue Proteins / genetics*
Pedigree
Seizures, Febrile / diagnosis,  genetics
Sodium Channels / genetics*
Chemical
Reg. No./Substance:
0/Nerve Tissue Proteins; 0/Sodium Channels; 0/sodium channel, voltage-gated, type I, alpha protein

From MEDLINE®/PubMed®, a database of the U.S. National Library of Medicine


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