Document Detail


Fibrodysplasia ossificans progressiva: report of two cases.
MedLine Citation:
PMID:  11138342     Owner:  NLM     Status:  MEDLINE    
Abstract/OtherAbstract:
Fibrodysplasia Ossificans Progressiva (FOP) is a rare hereditary connective tissue disease, genetically inherited as an autosomal dominant trait with complete penetrance but variable expressivity. Onset is typically in childhood and progressive involvement of the spine and proximal extremities leads to immobility and articular dysfunction. We present two cases with the typical features of FOP and a review of the pathogenesis, clinical manifestations and treatment options of this rare disease.
Authors:
J E Fonseca; J C Branco; J Reis; T Evangelista; V Tavares; A R Gomes; M V Queiroz
Publication Detail:
Type:  Case Reports; Journal Article; Review    
Journal Detail:
Title:  Clinical and experimental rheumatology     Volume:  18     ISSN:  0392-856X     ISO Abbreviation:  Clin. Exp. Rheumatol.     Publication Date:    2000 Nov-Dec
Date Detail:
Created Date:  2001-01-02     Completed Date:  2001-03-01     Revised Date:  2005-11-16    
Medline Journal Info:
Nlm Unique ID:  8308521     Medline TA:  Clin Exp Rheumatol     Country:  Italy    
Other Details:
Languages:  eng     Pagination:  749-52     Citation Subset:  IM    
Affiliation:
Rheumatology Unit, Santa Maria Hospital, Portugal. mop45465@mail.telepac.pt
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MeSH Terms
Descriptor/Qualifier:
Adolescent
Hip Joint / radiography
Humans
Male
Myositis Ossificans / etiology,  physiopathology,  radiography*,  therapy
Scoliosis / complications,  radiography
Spine / radiography

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