Document Detail


Familial case of Blau syndrome associated with a CARD15/NOD2 mutation.
MedLine Citation:
PMID:  20565245     Owner:  NLM     Status:  MEDLINE    
Abstract/OtherAbstract:
PURPOSE: Blau syndrome is a rare autosomal dominant disorder characterized by early onset granulomatous arthritis, uveitis, skin rash and camptodactyly. We report a familial case of Blau syndrome associated with a CARD15/NOD2 mutation. METHODS: PCR amplification and automated DNA sequencing of the complete CARD15/NOD2 coding sequence was performed. RESULTS: Molecular analysis in affected subjects disclosed a heterozygous c.1147G>C point mutation in CARD15/NOD2 exon 4, that predicts a p.E383K change at the protein level. CONCLUSIONS: Blau syndrome should be considered in the differential diagnosis of childhood uveitis and the genetic analysis of the CARD15/NOD2 gene is helpful in the diagnosis.
Authors:
Cristina Villanueva-Mendoza; Lourdes Arellanes-García; Victoria Cubas-Lorenzo; Maria C Jimenez-Martinez; Luis Felipe Flores-Suárez; Juan Carlos Zenteno
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Publication Detail:
Type:  Case Reports; Journal Article    
Journal Detail:
Title:  Ophthalmic genetics     Volume:  31     ISSN:  1744-5094     ISO Abbreviation:  Ophthalmic Genet.     Publication Date:  2010 Sep 
Date Detail:
Created Date:  2010-08-06     Completed Date:  2010-10-21     Revised Date:  -    
Medline Journal Info:
Nlm Unique ID:  9436057     Medline TA:  Ophthalmic Genet     Country:  England    
Other Details:
Languages:  eng     Pagination:  155-8     Citation Subset:  IM    
Affiliation:
Asociación para Evitar la Ceguera en México, Genetics, México City, Mexico. villanuevacristina@hotmail.com
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MeSH Terms
Descriptor/Qualifier:
Adult
Arthritis, Rheumatoid / genetics*
Exanthema / genetics*
Female
Fluorescein Angiography
Humans
Joint Diseases / genetics*
Nod2 Signaling Adaptor Protein / genetics*
Pedigree
Point Mutation*
Polymerase Chain Reaction
Recurrence
Syndrome
Uveitis, Anterior / genetics*
Young Adult
Chemical
Reg. No./Substance:
0/NOD2 protein, human; 0/Nod2 Signaling Adaptor Protein

From MEDLINE®/PubMed®, a database of the U.S. National Library of Medicine


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