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Effects of the histone deacetylase inhibitor ITF2357 in autoinflammatory syndromes.
MedLine Citation:
PMID:  21274502     Owner:  NLM     Status:  Publisher    
Abstract/OtherAbstract:
OBJECTIVE: We explored the effects of the oral histone deacetylase (HDAC) inhibitor ITF2357 in patients with autoinflammatory syndromes. METHODS: In this prospective open-label pilot study 8 patients were enrolled; One patient with Tumour Necrosis Factor Receptor Associated Periodic Syndrome (TRAPS), 3 patients with hyper-IgD and periodic fever syndrome (HIDS) and 4 patients with Schnitzler syndrome were closely followed during 90 days of ITF2357 treatment. RESULTS: Three patients with Schnitzler syndrome and 1 TRAPS patient experienced a partial remission. In 4 patients there was no effect. In HIDS patients there was a tendency towards a higher attack frequency and increasing attack severity. In 2 patients (1 TRAPS and 1 HIDS), we observed a decrease of acute phase response without signs of clinical improvement. One patient with Schnitzler syndrome showed a partial response despite an ongoing acute phase response. CONCLUSION: ITF2357 monotherapy was able to induce partial response only in patients with Schnitzler syndrome and no response in patients with HIDS.
Authors:
Evelien J Bodar; Anna Simon; Jos W M Van Der Meer
Publication Detail:
Type:  JOURNAL ARTICLE     Date:  2011-1-25
Journal Detail:
Title:  Molecular medicine (Cambridge, Mass.)     Volume:  -     ISSN:  1528-3658     ISO Abbreviation:  -     Publication Date:  2011 Jan 
Date Detail:
Created Date:  2011-1-28     Completed Date:  -     Revised Date:  -    
Medline Journal Info:
Nlm Unique ID:  9501023     Medline TA:  Mol Med     Country:  -    
Other Details:
Languages:  ENG     Pagination:  -     Citation Subset:  -    
Affiliation:
Department of General Internal Medicine and Nijmegen Institute for Infection, Inflammation, and Immunity (N4i), Radboud University Nijmegen Medical Centre, Nijmegen, The Netherlands.
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