Document Detail


Early onset of renal cancer in a family with Birt-Hogg-Dubé syndrome.
MedLine Citation:
PMID:  19320655     Owner:  NLM     Status:  MEDLINE    
Abstract/OtherAbstract:
Birt-Hogg-Dubé syndrome is a hereditary syndrome characterized by benign disease of skin and lungs and a risk of malignant renal tumors. We describe a clinical and genetic study of a large Dutch family with a novel mutation in the FLCN gene. Renal cancer at very young age occurred in one branch of this family, while in other branches, cutaneous and pulmonary symptoms predominated. A variety of congenital anomalies and connective tissue abnormalities were observed, possibly associated with the gene mutation.
Authors:
I Kluijt; D de Jong; H J Teertstra; P H Axwijk; J J P Gille; K Bell; A van Rens; A W G van der Velden; L Middelton; S Horenblas
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Publication Detail:
Type:  Case Reports; Journal Article     Date:  2009-03-23
Journal Detail:
Title:  Clinical genetics     Volume:  75     ISSN:  1399-0004     ISO Abbreviation:  Clin. Genet.     Publication Date:  2009 Jun 
Date Detail:
Created Date:  2009-06-10     Completed Date:  2009-10-05     Revised Date:  -    
Medline Journal Info:
Nlm Unique ID:  0253664     Medline TA:  Clin Genet     Country:  Denmark    
Other Details:
Languages:  eng     Pagination:  537-43     Citation Subset:  IM    
Affiliation:
Family Cancer Clinic, The Netherlands Cancer Institute/Antoni van Leeuwenhoek Hospital, Amsterdam, the Netherlands. i.kluijt@nki.nl
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MeSH Terms
Descriptor/Qualifier:
Adult
Age of Onset
Aged
Base Sequence
Carcinoma, Papillary / diagnosis,  epidemiology,  genetics
DNA / analysis
Family*
Female
Humans
Kidney Neoplasms / diagnosis*,  epidemiology,  genetics*
Lung Diseases / diagnosis,  genetics
Male
Middle Aged
Molecular Sequence Data
Pedigree
Pneumothorax / diagnosis,  genetics
Proto-Oncogene Proteins / genetics
Sequence Deletion
Skin Abnormalities / diagnosis,  genetics
Syndrome
Tumor Suppressor Proteins / genetics
Chemical
Reg. No./Substance:
0/FLCN protein, human; 0/Proto-Oncogene Proteins; 0/Tumor Suppressor Proteins; 9007-49-2/DNA

From MEDLINE®/PubMed®, a database of the U.S. National Library of Medicine


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