Document Detail


Deleterious mutations in SPINK5 in a patient with congenital ichthyosiform erythroderma: molecular testing as a helpful diagnostic tool for Netherton syndrome.
MedLine Citation:
PMID:  15347338     Owner:  NLM     Status:  MEDLINE    
Abstract/OtherAbstract:
The congenital erythrodermas represent a heterogeneous group of inherited and acquired disorders often accompanied by systemic infections, impaired epidermal barrier function and concomitant life-threatening fluid and electrolyte imbalance. In the present report, we describe a patient who was considered to have congenital ichthyosiform erythroderma for 26 years until molecular testing led to the correct diagnosis of Netherton syndrome.
Authors:
E Sprecher; A Tesfaye-Kedjela; P Ratajczak; R Bergman; G Richard
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Publication Detail:
Type:  Case Reports; Journal Article; Research Support, U.S. Gov't, P.H.S.    
Journal Detail:
Title:  Clinical and experimental dermatology     Volume:  29     ISSN:  0307-6938     ISO Abbreviation:  Clin. Exp. Dermatol.     Publication Date:  2004 Sep 
Date Detail:
Created Date:  2004-09-06     Completed Date:  2004-12-30     Revised Date:  2007-11-15    
Medline Journal Info:
Nlm Unique ID:  7606847     Medline TA:  Clin Exp Dermatol     Country:  England    
Other Details:
Languages:  eng     Pagination:  513-7     Citation Subset:  IM    
Affiliation:
Department of Dermatology and Laboratory of Molecular Dermatology, Rambam Medical Center, Haifa, Israel. e_sprecher@rambam.health.gov.il
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MeSH Terms
Descriptor/Qualifier:
Adult
Carrier Proteins / genetics*
DNA Mutational Analysis / methods
Dermatitis, Exfoliative / genetics,  pathology
Diagnosis, Differential
Hair / abnormalities*,  pathology
Humans
Ichthyosiform Erythroderma, Congenital / diagnosis*,  genetics
Ichthyosis / diagnosis*,  genetics,  pathology
Male
Mutation
Proteinase Inhibitory Proteins, Secretory
Syndrome
Grant Support
ID/Acronym/Agency:
AR38923/AR/NIAMS NIH HHS; AR47157/AR/NIAMS NIH HHS
Chemical
Reg. No./Substance:
0/Carrier Proteins; 0/Proteinase Inhibitory Proteins, Secretory; 0/SPINK5 protein, human

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