Document Detail


Clinical and histomolecular endometrial tumor characterization of patients at-risk for Lynch syndrome in South of Brazil.
MedLine Citation:
PMID:  19821155     Owner:  NLM     Status:  MEDLINE    
Abstract/OtherAbstract:
Lynch syndrome is an autosomal dominant cancer predisposition syndrome caused by germline mutations in one of the mismatch repair (MMR) genes: MLH1, MSH2, MSH6 and PMS2. Clinically, Lynch syndrome is characterized by early onset (45 years) of colorectal cancer (CRC), as well as extra-colonic cancer. Male and female carriers of Lynch syndrome-associated mutations have different lifetime risks for CRC and in women endometrial cancer (EC) may be the most common tumor. Whenever Amsterdam criteria are not fulfilled, the currently recommended laboratory screening strategies involve microsatellite instability testing and immunohistochemistry staining of the tumor for the major MMR proteins. The aim of this study was to estimate the frequency of MMR deficiencies in women diagnosed with EC who are at-risk for Lynch syndrome. Thirty women diagnosed with EC under the age of 50 years and/or women with EC and a first degree relative diagnosed with a Lynch syndrome-associated tumor were included. To assess MMR deficiencies four methods were used: multiplex PCR, Single Strand Conformation Polymorphism, Immunohistochemistry and Methylation Specific-Multiplex Ligation-dependent Probe Amplification. Twelve (40%) patients with EC fulfilling one of the inclusion criteria had results indicative of MMR deficiency. The identification of 5 women with clear evidence of MMR deficiency and absence of either Amsterdam or Bethesda criteria among 10 diagnosed with EC under the age of 50 years reinforces previous suggestions by some authors that these women should be considered at risk and always screened for Lynch syndrome after informed consent.
Authors:
Silvia Liliana Cossio; Patricia Koehler-Santos; Suzana Arenhart Pessini; Heleuza Mónego; Maria Isabel Edelweiss; Luise Meurer; Abdellatif Errami; Jordy Coffa; Hugo Bock; Maria Luiza Saraiva-Pereira; Patricia Ashton-Prolla; João Carlos Prolla
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Publication Detail:
Type:  Journal Article; Research Support, Non-U.S. Gov't    
Journal Detail:
Title:  Familial cancer     Volume:  9     ISSN:  1573-7292     ISO Abbreviation:  Fam. Cancer     Publication Date:  2010 Jun 
Date Detail:
Created Date:  2010-05-17     Completed Date:  2010-09-15     Revised Date:  -    
Medline Journal Info:
Nlm Unique ID:  100898211     Medline TA:  Fam Cancer     Country:  Netherlands    
Other Details:
Languages:  eng     Pagination:  131-9     Citation Subset:  IM    
Affiliation:
Programa de Pós-Graduação em Medicina: Ciências Gastroenterológicas, Universidade Federal do Rio Grande do Sul (UFRGS), Porto Alegre, RS, Brazil. slilianacossio@gmail.com
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MeSH Terms
Descriptor/Qualifier:
Brazil / epidemiology
Colorectal Neoplasms / epidemiology,  genetics,  physiopathology
Colorectal Neoplasms, Hereditary Nonpolyposis / diagnosis*,  etiology,  genetics
DNA Methylation / genetics
DNA Mismatch Repair / genetics*
DNA Repair
DNA-Binding Proteins / genetics
Endometrial Neoplasms / complications*,  epidemiology,  genetics
Female
Humans
Immunohistochemistry
Male
Microsatellite Instability*
MutS Homolog 2 Protein / genetics*
Risk
Chemical
Reg. No./Substance:
0/DNA-Binding Proteins; 0/G-T mismatch-binding protein; EC 3.6.1.3/MutS Homolog 2 Protein

From MEDLINE®/PubMed®, a database of the U.S. National Library of Medicine


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