Document Detail


Cervico-oculo-acusticus (Wildervanck's) syndrome: a clinical variant of Klippel-Feil sequence?
MedLine Citation:
PMID:  2355722     Owner:  NLM     Status:  MEDLINE    
Abstract/OtherAbstract:
A 7-year-old female child with phenotype of Cervico-Oculo-Acousticus (Wildervanck's) syndrome is presented. In addition to fusion of multiple cervical vertebrae with short neck, abducens nerve palsy and deafness, the child showed severe growth and bone delay, renal abnormalities and slight mental retardation. The presence of such malformations seems to suggest that Wildervanck's syndrome is a clinical variant of Klippel-Feil sequence. Both conditions usually have sporadic occurrence with female prevalence, more consistent for cervico-oculo-acousticus syndrome. The possibility of dominant inheritance has been postulated for both, autosomal for Klippel-Feil, autosomal or X-linked with lethality in hemizygous for Wildervank's one. An environmental etiology, due to a vascular disruption sequence during embryonic development, has been noted in Klippel-Feil, as in Moebius and Poland sequences. A combination of defects (Klippel-Feil and Moebius) could induce the more complex phenotype observed in Wildervanck's syndrome.
Authors:
G Corsello; A Carcione; L Castro; L Giuffrè
Publication Detail:
Type:  Case Reports; Journal Article    
Journal Detail:
Title:  Klinische Pädiatrie     Volume:  202     ISSN:  0300-8630     ISO Abbreviation:  Klin Padiatr     Publication Date:    1990 May-Jun
Date Detail:
Created Date:  1990-07-26     Completed Date:  1990-07-26     Revised Date:  2004-11-17    
Medline Journal Info:
Nlm Unique ID:  0326144     Medline TA:  Klin Padiatr     Country:  GERMANY, WEST    
Other Details:
Languages:  eng     Pagination:  176-9     Citation Subset:  IM    
Affiliation:
Istituto Materno-Infantile Università di Palermo.
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MeSH Terms
Descriptor/Qualifier:
Abnormalities, Multiple* / genetics
Child
Deafness / complications*,  genetics
Female
Genes, Dominant
Humans
Klippel-Feil Syndrome / complications*,  genetics
Ophthalmoplegia / complications,  genetics
Phenotype
Syndrome

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