Document Detail


Carrier testing in the fragile X syndrome: attitudes and opinions of obligate carriers.
MedLine Citation:
PMID:  8986278     Owner:  NLM     Status:  MEDLINE    
Abstract/OtherAbstract:
This study surveyed obligate carriers of the fragile X syndrome fra(X) to ascertain opinions and attitudes regarding carrier testing. Female carriers of fra(X) syndrome were recruited during their visits to the Fragile X Clinic at Duke University Medical Center. Twenty-eight obligate carriers completed a 48 question structured interview and a visual analog scale (VAS). Strong trends in the responses were identified. Fra(X) syndrome was viewed as a very serious problem and the risk to offspring high. Subjects reported that prior knowledge of carrier status would have changed their reproductive plans. All felt that relatives should be informed about the inheritance of fra(X) syndrome; the mean age given for preferred age to inform their children of the inheritance of fra(X) syndrome was 12 years, and mean age given for optimal timing of carrier testing was 10 years. The women interviewed indicated that growing up with knowledge of their carrier status would have been preferable to learning this information as adults and they endorsed an aggressive approach to informing and testing their children. Further investigation is warranted to determine the psychological consequences of carrier testing for fra(X) syndrome in order to develop appropriate guidelines for testing and informing individuals at risk for fra(X) syndrome.
Authors:
A McConkie-Rosell; G A Spiridigliozzi; T Iafolla; J Tarleton; A M Lachiewicz
Related Documents :
7811168 - Gustatory facial sweating subsequent to upper thoracic sympathectomy.
12494438 - Concurrence of fragile x syndrome and 47, xyy in an individual with a prader-willi-like...
3519008 - Does melatonin deficiency cause the enlarged genitalia of the fragile-x syndrome?
15748838 - Courting a cure for fragile x.
3547548 - Gilles de la tourette syndrome: etiologic considerations.
21048578 - Pharyngeal-cervical-brachial variant of guillain-barre syndrome in a patient with thala...
Publication Detail:
Type:  Journal Article    
Journal Detail:
Title:  American journal of medical genetics     Volume:  68     ISSN:  0148-7299     ISO Abbreviation:  Am. J. Med. Genet.     Publication Date:  1997 Jan 
Date Detail:
Created Date:  1997-03-18     Completed Date:  1997-03-18     Revised Date:  2004-11-17    
Medline Journal Info:
Nlm Unique ID:  7708900     Medline TA:  Am J Med Genet     Country:  UNITED STATES    
Other Details:
Languages:  eng     Pagination:  62-9     Citation Subset:  IM    
Affiliation:
Department of Pediatrics, Duke University Medical Center, Durham, North Carolina 27710, USA.
Export Citation:
APA/MLA Format     Download EndNote     Download BibTex
MeSH Terms
Descriptor/Qualifier:
Adult
Child
Female
Fragile X Syndrome / genetics,  psychology*
Health Knowledge, Attitudes, Practice*
Heterozygote Detection*
Humans
Male
Pain Measurement

From MEDLINE®/PubMed®, a database of the U.S. National Library of Medicine


Previous Document:  Diagnosis of Fanconi anemia in patients without congenital malformations: an international Fanconi A...
Next Document:  Tetramelic mirror-image polydactyly and a de novo balanced translocation between 2p23.3 and 14q13.