Document Detail


CADASIL presenting with a movement disorder: a clinical study of a Chilean kindred.
MedLine Citation:
PMID:  16538621     Owner:  NLM     Status:  MEDLINE    
Abstract/OtherAbstract:
Cerebral autosomal dominant arteriopathy with subcortical infarcts and leukoencephalopathy (CADASIL) is a hereditary vascular disease that usually begins with migraine, followed by repeated strokes and progressive dementia. We describe an unusual clinical presentation of this condition in members of a Chilean family with an established NOTCH3 mutation. We report early clinical, neuropsychological, transcranial ultrasound, magnetic resonance imaging (MRI), cerebral blood flow, and skin biopsy findings on these patients. Of the patients, 2 presented with facial dystonia, 1 of whom had abnormal single photon emission computed tomography and transcranial ultrasound studies after normal brain MRI scans. Our report emphasizes that CADASIL must be considered in the study of patients with secondary dystonia.
Authors:
Marcelo Miranda; Martin Dichgans; Andrea Slachevsky; Francisco Urbina; Ismael Mena; Pablo Venegas; Marcelo Galvez
Publication Detail:
Type:  Case Reports; Journal Article    
Journal Detail:
Title:  Movement disorders : official journal of the Movement Disorder Society     Volume:  21     ISSN:  0885-3185     ISO Abbreviation:  Mov. Disord.     Publication Date:  2006 Jul 
Date Detail:
Created Date:  2006-08-28     Completed Date:  2006-12-15     Revised Date:  -    
Medline Journal Info:
Nlm Unique ID:  8610688     Medline TA:  Mov Disord     Country:  United States    
Other Details:
Languages:  eng     Pagination:  1008-12     Citation Subset:  IM    
Copyright Information:
(c) 2006 Movement Disorder Society.
Affiliation:
Department of Neurology, Nuclear Medicine and Dermatology, Clinica Las Condes and Universidad de Chile, Santiago, Chile. marcelomiranda@terra.cl
Export Citation:
APA/MLA Format     Download EndNote     Download BibTex
MeSH Terms
Descriptor/Qualifier:
Adult
Aged
Biopsy
Brain / pathology
Brain Ischemia / diagnosis,  genetics
CADASIL / diagnosis,  genetics*
Cerebral Ventricles / pathology
Chile
DNA Mutational Analysis
Dementia / diagnosis,  genetics
Diagnosis, Differential
Diagnostic Imaging
Disease Progression
Endothelium, Vascular / pathology
Exons
Facial Muscles
Female
Follow-Up Studies
Gyrus Cinguli / pathology
Humans
Image Processing, Computer-Assisted
Imaging, Three-Dimensional
Male
Meige Syndrome / diagnosis,  genetics*
Microcirculation / pathology
Microscopy, Electron, Transmission
Neuropsychological Tests
Pedigree
Receptors, Notch / genetics*
Skin / blood supply,  pathology
Temporal Lobe / pathology
Chemical
Reg. No./Substance:
0/NOTCH3 protein, human; 0/Receptors, Notch

From MEDLINE®/PubMed®, a database of the U.S. National Library of Medicine


Previous Document:  Topography of putaminal degeneration in multiple system atrophy: a diffusion magnetic resonance stud...
Next Document:  Live imaging of fluorescent proteins in chordate embryos: from ascidians to mice.