Document Detail


Biphenotypic hematologic malignancy: a case report of the 8p11 myeloproliferative syndrome in a child.
MedLine Citation:
PMID:  20562652     Owner:  NLM     Status:  MEDLINE    
Abstract/OtherAbstract:
SUMMARY: The 8p11 myeloproliferative syndrome, also known as stem cell leukemia/lymphoma, is a rare, atypical, myeloproliferative disorder and lymphoid malignancy associated with chromosomal abnormalities involving the 8p11 chromosomal band. Translocations associated with this syndrome result in the fusion of the fibroblast growth factor receptor 1 (FGFR 1) gene with various partners, resulting in ligand-independent FGFR activity. To date, 8 partner genes have been identified in association with FGFR1 rearrangements. The most frequent FGFR1 translocation partner is the zinc finger gene ZNF198 located at 13q11. Disease phenotypes associated with this translocation include poor prognosis and transformation to acute leukemia and non-Hodgkin lymphoma. In common with a T-cell phenotype, obtaining and maintaining remission is difficult by conventional chemotherapy. This study describes an illustrative case of 8p11 myeloproliferative syndrome/stem cell leukemia/lymphoma outlining its chief features and historical developments.
Authors:
Xiangli Chen; Yin Zhang; Yulong Li; Pingchong Lei; Yaping Zhai; Linxiang Liu
Publication Detail:
Type:  Case Reports; Journal Article    
Journal Detail:
Title:  Journal of pediatric hematology/oncology     Volume:  32     ISSN:  1536-3678     ISO Abbreviation:  J. Pediatr. Hematol. Oncol.     Publication Date:  2010 Aug 
Date Detail:
Created Date:  2010-08-06     Completed Date:  2010-08-20     Revised Date:  2011-10-06    
Medline Journal Info:
Nlm Unique ID:  9505928     Medline TA:  J Pediatr Hematol Oncol     Country:  United States    
Other Details:
Languages:  eng     Pagination:  501-3     Citation Subset:  IM    
Affiliation:
Department of Clinical Hematology, Henan Provincial People's Hospital, First Hospital of Zhengzhou University, Zhengzhou, Henan Province, China.
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MeSH Terms
Descriptor/Qualifier:
Antineoplastic Combined Chemotherapy Protocols / therapeutic use
Child
Chromosomes, Human, Pair 13 / genetics*
Chromosomes, Human, Pair 8 / genetics*
Cyclophosphamide / therapeutic use
Dexamethasone / therapeutic use
Doxorubicin / therapeutic use
Etoposide / therapeutic use
Humans
Male
Myeloproliferative Disorders / congenital,  genetics*,  physiopathology
Phenotype
Precancerous Conditions / congenital,  genetics*
Precursor B-Cell Lymphoblastic Leukemia-Lymphoma / drug therapy,  genetics,  physiopathology
Precursor T-Cell Lymphoblastic Leukemia-Lymphoma / drug therapy,  genetics,  physiopathology
Prednisone / therapeutic use
Syndrome
Translocation, Genetic
Vincristine / therapeutic use
Chemical
Reg. No./Substance:
23214-92-8/Doxorubicin; 33419-42-0/Etoposide; 50-02-2/Dexamethasone; 50-18-0/Cyclophosphamide; 53-03-2/Prednisone; 57-22-7/Vincristine

From MEDLINE®/PubMed®, a database of the U.S. National Library of Medicine


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