Document Detail


Autoimmune hemolytic anemia in chronic mucocutaneous candidiasis.
MedLine Citation:
PMID:  7496919     Owner:  NLM     Status:  MEDLINE    
Abstract/OtherAbstract:
Chronic mucocutaneous candidiasis is an immunodeficiency disease characterized by T-cell dysregulation and chronic superficial candidal infections. We report on three patients with chronic mucocutaneous candidiasis who developed autoantibodies to erythrocytes. Our first patient, a 19-year-old female, developed autoimmune hemolytic anemia (AIHA) that required multiple courses of treatment, including corticosteroids, intravenous immunoglobulin, and danazol. During the last exacerbation of AIHA, intensive treatment with corticosteroids and intravenous immunoglobulin failed and yet the patient responded to plasmapheresis. Our second patient, a 21-year-old male, developed AIHA which responded to oral corticosteroid therapy. Our third patient, a 6-year-old female without evidence of hemolysis, was found to have erythrocyte autoantibodies on routine screening. These three patients had positive direct antiglobulin tests, and the first patient had both immunoglobulin G (IgG) and IgM erythrocyte autoantibodies, while the remaining two patients had only IgG autoantibody. This is the first report of the association of AIHA with chronic mucocutaneous candidiasis. We suggest that all patients with chronic mucocutaneous candidiasis be screened periodically for erythrocyte autoantibodies. Plasmapheresis, a safe ancillary procedure in the management of AIHA, may be life-saving in some cases. The occurrence of erythrocyte autoantibodies in mucocutaneous candidiasis may be related to immunoregulatory disorders in this disease.
Authors:
B I Oyefara; H C Kim; R N Danziger; M Carroll; J M Greene; S D Douglas
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Publication Detail:
Type:  Case Reports; Journal Article    
Journal Detail:
Title:  Clinical and diagnostic laboratory immunology     Volume:  1     ISSN:  1071-412X     ISO Abbreviation:  Clin. Diagn. Lab. Immunol.     Publication Date:  1994 Jan 
Date Detail:
Created Date:  1996-01-16     Completed Date:  1996-01-16     Revised Date:  2009-11-18    
Medline Journal Info:
Nlm Unique ID:  9421292     Medline TA:  Clin Diagn Lab Immunol     Country:  UNITED STATES    
Other Details:
Languages:  eng     Pagination:  38-43     Citation Subset:  IM    
Affiliation:
Division of Allergy, Immunology and Infectious Disease, Children's Hospital of Philadelphia, PA 19104, USA.
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MeSH Terms
Descriptor/Qualifier:
Adolescent
Adult
Anemia, Hemolytic, Autoimmune / blood,  complications*,  immunology
Autoantibodies / biosynthesis*
Candidiasis, Chronic Mucocutaneous / blood,  complications*,  immunology
Child
Erythrocytes / immunology*
Female
Humans
Male
Chemical
Reg. No./Substance:
0/Autoantibodies
Comments/Corrections

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