Document Detail


Analysis of the A(TA)(n)TAA configuration in the promoter region of the UGT1 A1 gene in Greek patients with thalassemia intermedia and sickle cell disease.
MedLine Citation:
PMID:  12850481     Owner:  NLM     Status:  MEDLINE    
Abstract/OtherAbstract:
Gilbert's syndrome is characterized by mild unconjugated hyperbilirubinemia. The molecular basis of this syndrome usually concerns an additional dinucleotide insertion (TA) in the A(TA)(n)TAA configuration residing in the promoter region of the UGT1 A1 gene. This configuration may vary in length; the "n" represents the different number of TA repeats. The homozygosity A(TA)(7)TAA/A(TA)(7)TAA is involved in Gilbert's syndrome. In many cases of patients with thalassemia intermedia and sickle cell disease considerable variation in bilirubin levels is observed. In this study we investigated the contribution of the A(TA)(7)TAA/A(TA)(7)TAA genotype in the variable unconjugated serum bilirubin levels in 31 Greek patients with thalassemia intermedia and 27 Greek compound heterozygotes for beta thalassemia and sickle cell anemia. Analysis of the A(TA)(n)TAA configuration in the promoter region of the latter patients showed that those who were carrying the homozygosity A(TA)(7)TAA/A(TA)(7)TAA had higher levels of unconjugated bilirubin. These findings suggest that the coexistence of Gilbert's syndrome in patients with thalassemia intermedia and sickle cell disease may be the cause of the elevated values of unconjugated bilirubin, reducing the possibility of excessive hemolysis in these patients.
Authors:
Vassiliki Kalotychou; Katerina Antonatou; Revekka Tzanetea; Evaggelos Terpos; Dimitris Loukopoulos; Yannis Rombos
Publication Detail:
Type:  Journal Article    
Journal Detail:
Title:  Blood cells, molecules & diseases     Volume:  31     ISSN:  1079-9796     ISO Abbreviation:  Blood Cells Mol. Dis.     Publication Date:    2003 Jul-Aug
Date Detail:
Created Date:  2003-07-09     Completed Date:  2004-04-30     Revised Date:  2008-11-21    
Medline Journal Info:
Nlm Unique ID:  9509932     Medline TA:  Blood Cells Mol Dis     Country:  United States    
Other Details:
Languages:  eng     Pagination:  38-42     Citation Subset:  IM    
Affiliation:
First Department of Medicine, University of Athens School of Medicine, Laikon General Hospital, 11527, Athens, Greece. vkalotyc@med.uoa.gr
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MeSH Terms
Descriptor/Qualifier:
Amino Acid Sequence
Anemia, Sickle Cell / blood,  complications,  genetics*
Bilirubin / blood
Genotype
Gilbert Disease / complications,  genetics
Glucuronosyltransferase / genetics*
Greece
Humans
Hyperbilirubinemia / etiology,  genetics
Poly dA-dT / genetics*
Promoter Regions, Genetic*
Thalassemia / blood,  complications,  genetics*
Chemical
Reg. No./Substance:
26966-61-0/Poly dA-dT; 635-65-4/Bilirubin; EC 2.4.1.-/bilirubin uridine-diphosphoglucuronosyl transferase 1A1; EC 2.4.1.17/Glucuronosyltransferase

From MEDLINE®/PubMed®, a database of the U.S. National Library of Medicine


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