Document Detail


Alpha-1-antitrypsin deficiency panniculitis.
MedLine Citation:
PMID:  18793976     Owner:  NLM     Status:  MEDLINE    
Abstract/OtherAbstract:
Alpha-1-antitrypsin deficiency is a congenital error of metabolism linked to pulmonary (emphysema) and liver (cirrhosis) disease. Since 1972, panniculitis has been associated with this deficiency, initially related to Weber-Christian syndrome and finally as a differentiated entity. Clinical manifestations typically consist of wide nodular lesions on the trunk and proximal extremities that evolve to ulceration and drainage. Histopathologically it presents as a mixed septal-lobular panniculitis pattern with some typical findings referred. Differential diagnosis from other types of panniculitis and neutrophilic dermatosis must be established. Different treatments, including tetracyclines, dapsone, and alpha-1-antitrypsin repositioning, have shown variable efficacy in controlling this disease.
Authors:
Ricardo Valverde; Belén Rosales; Francisco Javier Ortiz-de Frutos; José Luis Rodríguez-Peralto; Pablo L Ortiz-Romero
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Publication Detail:
Type:  Journal Article; Review    
Journal Detail:
Title:  Dermatologic clinics     Volume:  26     ISSN:  0733-8635     ISO Abbreviation:  Dermatol Clin     Publication Date:  2008 Oct 
Date Detail:
Created Date:  2008-09-16     Completed Date:  2008-12-09     Revised Date:  -    
Medline Journal Info:
Nlm Unique ID:  8300886     Medline TA:  Dermatol Clin     Country:  United States    
Other Details:
Languages:  eng     Pagination:  447-51, vi     Citation Subset:  IM    
Affiliation:
"Hospital Universitario Doce de Octubre", Universidad Complutense, Madrid, Spain.
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MeSH Terms
Descriptor/Qualifier:
Diagnosis, Differential
Humans
Panniculitis / diagnosis,  etiology*,  metabolism
Phenotype
Skin / pathology*
alpha 1-Antitrypsin / genetics,  metabolism*
alpha 1-Antitrypsin Deficiency / complications*,  genetics,  metabolism
Chemical
Reg. No./Substance:
0/SERPINA1 protein, human; 0/alpha 1-Antitrypsin

From MEDLINE®/PubMed®, a database of the U.S. National Library of Medicine


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