Document Detail


Acrochordons are not a component of the Birt-Hogg-Dubé syndrome: does this syndrome exist? Case reports and review of the literature.
MedLine Citation:
PMID:  10446780     Owner:  NLM     Status:  MEDLINE    
Abstract/OtherAbstract:
Multiple fibrofolliculomas, trichodiscomas, and acrochordons compose the triad of cutaneous lesions characterizing the Birt-Hogg-Dubé syndrome, inherited in an autosomal dominant fashion. We report a case of a family who had the triad of tumors of the Birt-Hogg-Dubé syndrome. Two members were observed clinically and histologically. Biopsies of the facial papules disclosed features of the fibrofolliculoma/trichodiscoma spectrum. Lesions that were clinically acrochordon-like proved to correspond to the same histopathologic spectrum. The characterization of the nature of the acrochordon-like lesions in our patients and the review of the literature allow us to question if acrochordons (skin tags) should be maintained as a component of this association. In light of our conclusion that fibrofolliculoma, trichodiscoma, and the acrochordon-like lesions are histologic variations of a single lesion, we further question whether the term "syndrome" is valid.
Authors:
C De la Torre; C Ocampo; I G Doval; A Losada; M J Cruces
Publication Detail:
Type:  Case Reports; Journal Article; Review    
Journal Detail:
Title:  The American Journal of dermatopathology     Volume:  21     ISSN:  0193-1091     ISO Abbreviation:  Am J Dermatopathol     Publication Date:  1999 Aug 
Date Detail:
Created Date:  1999-09-17     Completed Date:  1999-09-17     Revised Date:  2005-11-16    
Medline Journal Info:
Nlm Unique ID:  7911005     Medline TA:  Am J Dermatopathol     Country:  UNITED STATES    
Other Details:
Languages:  eng     Pagination:  369-74     Citation Subset:  IM    
Affiliation:
Service of Dermatology, Hospital Provincial, Pontevedra, Spain.
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MeSH Terms
Descriptor/Qualifier:
Female
Fibroma / genetics,  pathology*
Hair Follicle / pathology
Hamartoma / pathology*
Humans
Male
Middle Aged
Neoplasms, Multiple Primary / genetics,  pathology*
Skin Neoplasms / genetics,  pathology*
Syndrome
Comments/Corrections
Comment In:
Am J Dermatopathol. 2000 Jun;22(3):293-4   [PMID:  10871079 ]

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